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SMAD4 幼年性息肉综合征和遗传性出血性毛细血管扩张症表现为中年男性的巨大蕈状胃肿块、上消化道和下消化道多发性息肉和缺铁性贫血,无已知家族史。

SMAD4 juvenile polyposis syndrome and hereditary haemorrhagic telangiectasia presenting in a middle-aged man as a large fungating gastric mass, polyposis in both upper and lower GI tract and iron deficiency anaemia, with no known family history.

机构信息

General Surgery, Mackay Base Hospital, Mackay, Queensland, Australia

Pathology, Queensland Pathology, Herston, Queensland, Australia.

出版信息

BMJ Case Rep. 2020 Dec 22;13(12):e236855. doi: 10.1136/bcr-2020-236855.

Abstract

Juvenile polyposis syndrome (JPS) and hereditary haemorrhagic telangiectasia (HHT) are rare autosomal dominant diseases, where symptoms manifest at childhood. A 32-year-old man with no family history of JPS or HHT with SMAD4 gene mutation who developed signs and symptoms only at the age of 32, when he was an adult. In this article, we highlight the steps taken to diagnose this rare pathology, explain its pathophysiology and management.

摘要

青少年息肉综合征(JPS)和遗传性出血性毛细血管扩张症(HHT)是罕见的常染色体显性疾病,其症状在儿童期表现出来。本文报道了一例 SMAD4 基因突变但无 JPS 或 HHT 家族史的 32 岁男性,直到 32 岁成年时才出现症状和体征。本文重点介绍了诊断这种罕见疾病的步骤,解释了其病理生理学和管理方法。

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引用本文的文献

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