General Surgery, Mackay Base Hospital, Mackay, Queensland, Australia
Pathology, Queensland Pathology, Herston, Queensland, Australia.
BMJ Case Rep. 2020 Dec 22;13(12):e236855. doi: 10.1136/bcr-2020-236855.
Juvenile polyposis syndrome (JPS) and hereditary haemorrhagic telangiectasia (HHT) are rare autosomal dominant diseases, where symptoms manifest at childhood. A 32-year-old man with no family history of JPS or HHT with SMAD4 gene mutation who developed signs and symptoms only at the age of 32, when he was an adult. In this article, we highlight the steps taken to diagnose this rare pathology, explain its pathophysiology and management.
青少年息肉综合征(JPS)和遗传性出血性毛细血管扩张症(HHT)是罕见的常染色体显性疾病,其症状在儿童期表现出来。本文报道了一例 SMAD4 基因突变但无 JPS 或 HHT 家族史的 32 岁男性,直到 32 岁成年时才出现症状和体征。本文重点介绍了诊断这种罕见疾病的步骤,解释了其病理生理学和管理方法。