与血管球瘤相关的单侧下肢萎缩：一例报告

Unilateral lower limb atrophy associated with glomus tumors: a case report.

作者信息

Akechi Yuji, Miura Shiroh, Ochi Masayuki, Enoki Moe, Matsuda Takuya, Kitazawa Riko, Fujibuchi Taketsugu, Ochi Hirofumi, Igase Michiya, Ohyagi Yasumasa

机构信息

Department of Neurology and Geriatric Medicine, Ehime University Graduate School of Medicine, Shitsukawa, Toon, Ehime, 791-0295, Japan.

Department of Radiology, Ehime University Graduate School of Medicine, Toon, Ehime, Japan.

出版信息

J Med Case Rep. 2021 Jan 13;15(1):8. doi: 10.1186/s13256-020-02616-1.

DOI:10.1186/s13256-020-02616-1

PMID:33436045

原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC7805226/

Abstract

BACKGROUND

Glomus tumors are soft tissue neoplasms comprised of glomus cells, vasculature, and smooth muscle cells, which occur commonly in a single subungual area of the digits, and their main clinical features include severe paroxysmal pain, localized tenderness, and cold hypersensitivity.

CASE PRESENTATION

A 47-year-old Japanese man had suffered from chronic progressive paroxysmal shooting pain in his right leg since childhood. He avoided putting weight on his right foot whenever he walked. The frequency of paroxysmal pain and the number of tender points both gradually increased with age, and his right leg gradually atrophied. Magnetic resonance imaging of the lower extremity demonstrated multiple gadolinium-enhanced nodules that corresponded with his tender points. Excisional biopsy relieved his pain and provided a histopathological diagnosis of glomus tumors.

CONCLUSION

This case suggests that small glomus tumors located in deep tissue may cause disuse atrophy because of their long delay before diagnosis. Clinicians should consider the potential for glomus tumors when patients exhibit unilateral lower limb muscular atrophy with pain.

摘要