Department of Urology, The Children's Hospital, Zhejiang University School of Medicine, National Clinical Research Center for Child Health, Hangzhou, China.
The Children's Hospital, Zhejiang University School of Medicine, National Clinical Research Center for Child Health, National Children's Regional Medical Center, Hangzhou, China.
Andrologia. 2022 Mar;54(2):e14292. doi: 10.1111/and.14292. Epub 2021 Oct 26.
A variety of mutations in the androgen receptor (AR) gene are linked to androgen insensitivity syndrome (AIS). AIS is the most common specific cause of 46, XY disorder in sex development. Here, we reported a patient which presented as a female with 46, XY karyotype and normal female external genitalia. The patient was diagnosed with complete AIS caused by a novel mutation (NM_000044, c.2678-2726del, p. Pro893Leufs*35) in the AR gene. Targeted exome sequencing was used to detect the patient's androgen receptor gene mutations. Sanger sequencing was used to validate the mutation. This study showed that a novel mutation of the AR gene can cause complete AIS; the study also broadened the AR mutation spectrum and indicated that targeted exome sequencing could help facilitate the diagnosis of complicated disorders in sexual development.
雄激素受体(AR)基因突变与雄激素不敏感综合征(AIS)有关。AIS 是性发育 46,XY 障碍最常见的特定原因。在这里,我们报告了一名患者,其核型为 46,XY,外生殖器正常,表现为女性。该患者被诊断为完全 AIS,由 AR 基因中的新型突变(NM_000044,c.2678-2726del,p.Pro893Leufs*35)引起。使用靶向外显子组测序检测患者的雄激素受体基因突变。Sanger 测序用于验证突变。本研究表明 AR 基因突变可导致完全 AIS;该研究还拓宽了 AR 突变谱,并表明靶向外显子组测序有助于促进性发育复杂疾病的诊断。