Department of Neurosurgery, Washington University in St. Louis School of Medicine, St. Louis, Missouri, USA.
Neurol India. 2021 Nov-Dec;69(Supplement):S268-S274. doi: 10.4103/0028-3886.332249.
Hydrocephalus is a neurological disorder with an incidence of 80-125 per 100,000 live births in the United States. The molecular pathogenesis of this multidimensional disorder is complex and has both genetic and environmental influences. This review aims to discuss the genetic and molecular alterations described in human hydrocephalus, from well-characterized, heritable forms of hydrocephalus (e.g., X-linked hydrocephalus from L1CAM variants) to those affecting cilia motility and other complex pathologies such as neural tube defects and Dandy-Walker syndrome. Ventricular zone disruption is one key pattern among congenital and acquired forms of hydrocephalus, with abnormalities in cadherins, which mediate neuroepithelium/ependymal cell junctions and contribute to the pathogenesis and severity of the disease. Given the relationship between hydrocephalus pathogenesis and neurodevelopment, future research should elucidate the genetic and molecular mechanisms that regulate ventricular zone integrity and stem cell biology.
脑积水是一种神经疾病,在美国的发病率为每 10 万活产儿中有 80-125 例。这种多维疾病的分子发病机制复杂,既有遗传因素,也有环境影响。本综述旨在讨论人类脑积水中描述的遗传和分子改变,从特征明确的、可遗传的脑积水形式(例如,来自 L1CAM 变体的 X 连锁脑积水)到影响纤毛运动和其他复杂病理的形式,如神经管缺陷和 Dandy-Walker 综合征。脑室区破坏是先天性和获得性脑积水的一种主要模式,钙黏蛋白异常,钙黏蛋白介导神经上皮/室管膜细胞连接,并有助于疾病的发病机制和严重程度。鉴于脑积水发病机制与神经发育之间的关系,未来的研究应该阐明调节脑室区完整性和干细胞生物学的遗传和分子机制。