Group of Applied Clinical Research in Hematology, Hospital del Mar Medical Research Institute (IMIM), Barcelona, Spain.
Pompeu Fabra University, Barcelona, Spain.
Blood Adv. 2022 May 24;6(10):3178-3188. doi: 10.1182/bloodadvances.2021006565.
Molecular and cytogenetic studies are essential for diagnosis and prognosis in patients with myelodysplastic syndromes (MDSs). Cell-free DNA (cfDNA) analysis has been reported to be a reliable noninvasive approach for detecting molecular abnormalities in MDS; however, there is limited information about cytogenetic alterations and monitoring in cfDNA. We assessed the molecular and cytogenetic profile of a cohort of 70 patients with MDS by next-generation sequencing (NGS) of cfDNA and compared the results to sequencing of paired bone marrow (BM) DNA. Sequencing of BM DNA and cfDNA showed a comparable mutational profile (92.1% concordance), and variant allele frequencies (VAFs) strongly correlated between both sample types. Of note, SF3B1 mutations were detected with significantly higher VAFs in cfDNA than in BM DNA. NGS and microarrays were highly concordant in detecting chromosomal alterations although with lower sensitivity than karyotype and fluorescence in situ hybridization. Nevertheless, all cytogenetic aberrations detected by NGS in BM DNA were also detected in cfDNA. In addition, we monitored molecular and cytogenetic alterations and observed an excellent correlation between the VAFs of mutations in BM DNA and cfDNA across multiple matched time points. A decrease in the cfDNA VAFs was detected in patients responding to therapy, but not in nonresponding patients. Of note, cfDNA analysis also showed cytogenetic evolution in 2 nonresponsive cases. In summary, although further studies with larger cohorts are needed, our results support the analysis of cfDNA as a promising strategy for performing molecular characterization, detection of chromosomal aberrations and monitoring of patients with MDS.
分子和细胞遗传学研究对于骨髓增生异常综合征(MDSs)患者的诊断和预后至关重要。已有研究报道,游离细胞 DNA(cfDNA)分析是一种可靠的非侵入性方法,可用于检测 MDS 中的分子异常;然而,关于 cfDNA 中的细胞遗传学改变和监测的信息有限。我们通过下一代测序(NGS)对 70 例 MDS 患者的 cfDNA 进行了分子和细胞遗传学分析,并将结果与配对骨髓(BM)DNA 的测序结果进行了比较。BM DNA 和 cfDNA 的测序显示出相似的突变谱(92.1%的一致性),两种样本类型的变异等位基因频率(VAFs)高度相关。值得注意的是,SF3B1 突变在 cfDNA 中的 VAF 明显高于 BM DNA。虽然与核型和荧光原位杂交相比,NGS 和微阵列在检测染色体改变方面的灵敏度较低,但它们在检测染色体改变方面高度一致。尽管如此,在 BM DNA 中通过 NGS 检测到的所有细胞遗传学异常也在 cfDNA 中检测到。此外,我们监测了分子和细胞遗传学改变,并观察到 BM DNA 和 cfDNA 中突变的 VAF 之间具有极好的相关性,在多个匹配的时间点均如此。在对治疗有反应的患者中,cfDNA 的 VAF 降低,但在无反应的患者中则没有。值得注意的是,cfDNA 分析还显示了 2 例无反应病例中的细胞遗传学演变。总之,尽管需要进一步进行更大队列的研究,但我们的结果支持将 cfDNA 分析作为一种很有前途的策略,用于进行分子特征分析、检测染色体异常和监测 MDS 患者。