Kounis Ilias, Lewin Maïté, Laurent-Bellue Astrid, Poli Edoardo, Coilly Audrey, Duclos-Vallée Jean-Charles, Guettier Catherine, Adam René, Lerut Jan, Samuel Didier, Rosmorduc Olivier
AP-HP Hôpital Paul Brousse, Centre Hépato-Biliaire, Villejuif, France.
FHU Hepatinov, Centre Hépato-Biliaire, Villejuif, France.
Ther Adv Med Oncol. 2022 Mar 23;14:17588359221086909. doi: 10.1177/17588359221086909. eCollection 2022.
In this article, we describe the case of a 34-year-old woman presenting a multifocal and metastatic epithelioid hemangioendothelioma (HEHE) of the liver. Under classical chemotherapy using cyclophosphamide, there was a fast tumor progression in liver and extra-hepatic metastatic sites (lungs and mediastinal lymph node). Taking into account the patient's age and the natural history of the HEHE, our goal was to try to bring her to liver transplantation (LT) and lenvatinib was an acceptable candidate for this reason. Shortly after the initiation of lenvatinib before LT and surgery, we observed the enlargement of large devascularized necrotic areas in most of the liver HEHE masses, suggesting a good response. The patient was finally transplanted 6 months after initiation of lenvatinib treatment. Eight months after LT, progression occurred (ascites, peritoneal recurrence, and mediastinal lymph node). After restarting lenvatinib, ascites disappeared and the lymph node decreased in size, suggesting a good response, more than 1 year after her transplantation. This is the first case report to our knowledge that illustrates the benefit of lenvatinib as a neoadjuvant bridge until LT for a multifocal and metastatic HEHE. In addition, this drug has also shown a benefit in term of disease control after a late recurrence of the tumor. We suggest that lenvatinib should be proposed as a bridge to the LT for nonresectable HEHE. Moreover, this drug was also beneficial in the treatment of late recurrence after LT. The absence of pharmacologic interactions between classical immunosuppressive drugs and lenvatinib may allow its use as an early adjuvant approach when the risk of recurrence is high. The strength of our case consists in the long follow-up and the innovative message allowing changing palliative strategies into curative ones in case of advanced HEHE.
在本文中,我们描述了一名34岁女性患有肝脏多灶性转移性上皮样血管内皮瘤(HEHE)的病例。在使用环磷酰胺的传统化疗下,肝脏和肝外转移部位(肺和纵隔淋巴结)出现了快速的肿瘤进展。考虑到患者的年龄和HEHE的自然病程,我们的目标是尝试为她进行肝移植(LT),基于这个原因,乐伐替尼是一个可接受的选择。在LT和手术前开始使用乐伐替尼后不久,我们观察到大多数肝脏HEHE肿块中大片去血管化坏死区域增大,提示反应良好。患者在开始乐伐替尼治疗6个月后最终接受了移植。LT后8个月,病情进展(腹水、腹膜复发和纵隔淋巴结转移)。重新开始使用乐伐替尼后,腹水消失,淋巴结缩小,提示反应良好,这发生在她移植后1年多。据我们所知,这是首例说明乐伐替尼作为多灶性转移性HEHE肝移植前新辅助桥梁的益处的病例报告。此外,这种药物在肿瘤晚期复发后的疾病控制方面也显示出益处。我们建议乐伐替尼应被用作不可切除HEHE肝移植的桥梁。而且,这种药物在LT后晚期复发的治疗中也有益处。传统免疫抑制药物与乐伐替尼之间不存在药物相互作用,这可能使其在复发风险高时可作为早期辅助方法使用。我们病例的优势在于长期随访以及传递了创新信息,即在晚期HEHE病例中可将姑息治疗策略转变为治愈性策略。