Farswan Akanksha, Gupta Anubha, Jena Lingaraja, Ruhela Vivek, Kaur Gurvinder, Gupta Ritu
SBILab, Department of ECE, Indraprastha Institute of Information Technology-Delhi (IIIT-Delhi) New Delhi 110020, India.
Laboratory Oncology Unit, Dr. B.R.A. IRCH, AIIMS New Delhi 110029, India.
Am J Cancer Res. 2022 Apr 15;12(4):1919-1933. eCollection 2022.
Mutational Signatures and Tumor mutational burden (TMB) have emerged as prognostic biomarkers in cancer genomics. However, the association of TMB with overall survival (OS) is still unknown in newly diagnosed multiple myeloma (NDMM) patients. Further, the change in the mutational spectrum involving both synonymous and non-synonymous mutations as MGUS progresses to MM is unexplored. This study addresses both these aspects via extensive evaluation of the mutations in MGUS and NDMM. WES data of 1018 NDMM patients and 61 MGUS patients collected from three different global regions were analyzed in this study. Single base substitutions, mutational signatures and TMB were inferred from the variants identified in MGUS and MM patients. The cutoff value for TMB was estimated to divide patients into low TMB and high TMB (hypermutators) groups. This study finds a change in the mutational spectrum with a statistically significant increase from MGUS to MM. There was a statistically significant increase in the frequency of all the three categories of variants, non-synonymous (NS), synonymous (SYN), and others (OTH), from MGUS to MM (P<0.05). However, there was a statistically significant rise in the TMB values for TMB_NS and TMB_SYN only. We also observed that 3' and 5'UTR mutations were more frequent in MM and might be responsible for driving MGUS to MM via regulatory binding sites. NDMM patients were also examined separately along with their survival outcomes. The frequency of hypermutators was low in MM with poor OS and PFS outcome. We observed a statistically significant rise in the frequency of C>A and C>T substitutions and a statistically significant decline in T>G substitutions in the MM patients with poor outcomes. Additionally, there was a statistically significant increase in the TMB of the patients with poor outcome compared to patients with a superior outcome. A statistically significant association between the APOBEC activity and poor overall survival in MM was discovered. These findings have potential clinical relevance and can assist in designing risk-adapted therapies to inhibit the progression of MGUS to MM and prolong the overall survival in high-risk MM patients.
突变特征和肿瘤突变负荷(TMB)已成为癌症基因组学中的预后生物标志物。然而,在新诊断的多发性骨髓瘤(NDMM)患者中,TMB与总生存期(OS)的关联仍不清楚。此外,随着意义未明的单克隆丙种球蛋白病(MGUS)进展为骨髓瘤(MM),涉及同义突变和非同义突变的突变谱变化尚未得到探索。本研究通过对MGUS和NDMM中的突变进行广泛评估来解决这两个方面的问题。本研究分析了从全球三个不同地区收集的1018例NDMM患者和61例MGUS患者的全外显子组测序(WES)数据。从MGUS和MM患者中鉴定出的变异推断出单碱基替换、突变特征和TMB。估计TMB的临界值以将患者分为低TMB组和高TMB(超突变体)组。本研究发现突变谱发生了变化,从MGUS到MM有统计学显著增加。从MGUS到MM,所有三类变异,即非同义(NS)、同义(SYN)和其他(OTH)的频率均有统计学显著增加(P<0.05)。然而,仅TMB_NS和TMB_SYN的TMB值有统计学显著升高。我们还观察到3'和5'非翻译区(UTR)突变在MM中更常见,可能通过调控结合位点促使MGUS进展为MM。还对NDMM患者及其生存结果进行了单独检查。在OS和无进展生存期(PFS)结果较差的MM中,超突变体的频率较低。我们观察到,预后较差的MM患者中,C>A和C>T替换的频率有统计学显著升高,而T>G替换有统计学显著下降。此外,与预后较好的患者相比,预后较差的患者的TMB有统计学显著增加。发现APOBEC活性与MM患者较差的总生存期之间存在统计学显著关联。这些发现具有潜在的临床相关性,可有助于设计风险适应性疗法,以抑制MGUS进展为MM,并延长高危MM患者的总生存期。