Jenkins Kathy J, Fineman Jeffrey R
Department of Cardiology, Boston Children's Hospital, Boston, MA 02115, USA.
Department of Pediatrics, University of California, San Francisco, CA 94143, USA.
Children (Basel). 2022 May 29;9(6):799. doi: 10.3390/children9060799.
Pulmonary vein stenosis (PVS) is a rare and poorly understood condition that can be classified as primary, acquired, status-post surgical repair of PVS, and/or associated with developmental lung disease. Immunohistochemical studies demonstrate that obstruction of the large (extrapulmonary) pulmonary veins is associated with the neointimal proliferation of myofibroblasts. This rare disorder is likely multifactorial with a spectrum of pathobiology. Treatments have been historically surgical, with an increasing repetitive interventional approach. Understanding the biology of these disorders is in its infancy; thus, medical management has lagged behind. Throughout medical history, an increased understanding of the underlying biology of a disorder has led to significant improvements in care and outcomes. One example is the treatment of pulmonary arterial hypertension (PAH). PAH shares several common themes with PVS. These include the spectrum of disease and biological alterations, such as vascular remodeling and vasoconstriction. Over the past two decades, an exponential increase in the understanding of the pathobiology of PAH has led to a dramatic increase in medical therapies that have changed the landscape of the disease. We believe that a similar approach to PVS can generate novel medical therapeutic targets that will markedly improve the outcome of these vulnerable patients.
肺静脉狭窄(PVS)是一种罕见且了解甚少的病症,可分为原发性、后天性、PVS手术后状态和/或与发育性肺病相关。免疫组织化学研究表明,大的(肺外)肺静脉阻塞与肌成纤维细胞的新生内膜增殖有关。这种罕见的疾病可能是多因素的,具有一系列病理生物学特征。治疗方法历来以手术为主,现在越来越多地采用重复性介入方法。对这些疾病生物学的了解尚处于起步阶段;因此,药物治疗滞后。在整个医学史上,对一种疾病潜在生物学的深入了解已导致护理和治疗结果的显著改善。一个例子是肺动脉高压(PAH)的治疗。PAH与PVS有几个共同主题。这些包括疾病谱和生物学改变,如血管重塑和血管收缩。在过去二十年中,对PAH病理生物学的理解呈指数级增长,导致了医学治疗方法的大幅增加,改变了该疾病的格局。我们相信,对PVS采用类似方法可以产生新的医学治疗靶点,这将显著改善这些脆弱患者的治疗结果。