Department of Neurological Surgery, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Sciences.
Departments of Pediatrics, Okayama University Hospital.
Acta Med Okayama. 2023 Jun;77(3):323-330. doi: 10.18926/AMO/65502.
In the current World Health Organization classification of central nervous system tumors, comprehensive genetic and epigenetic analyses are considered essential for precise diagnosis. A 14-year-old male patient who presented with a cerebellar tumor was initially diagnosed with glioblastoma and treated with radiation and concomitant temozolomide chemotherapy after resection. During maintenance temozolomide therapy, a new contrast-enhanced lesion developed in the bottom of the cavity formed by the resection. A second surgery was performed, but the histological findings in specimens from the second surgery were different from those of the first surgery. Although genome-wide DNA methylation profiling was conducted using frozen tissue for a precise diagnosis, the proportion of tumor cells was insufficient and only normal cerebellum was observed. We then performed comprehensive genetic analysis using formalin-fixed paraffin-embedded sections, which revealed MYCN amplification without alteration of IDH1, IDH2, or Histone H3. Finally, the patient was diagnosed with pediatric-type diffuse high-grade glioma, H3-wildtype and IDH-wildtype. In conclusion, comprehensive genetic and epigenetic analysis should be considered in pediatric brain tumor cases.
在目前的世界卫生组织中枢神经系统肿瘤分类中,全面的遗传和表观遗传分析被认为是精确诊断所必需的。一名 14 岁男性患者因小脑肿瘤就诊,最初被诊断为胶质母细胞瘤,在切除后接受了放疗和替莫唑胺化疗的联合治疗。在维持替莫唑胺治疗期间,在切除形成的腔底部出现了新的增强对比病变。进行了第二次手术,但第二次手术标本的组织学发现与第一次手术不同。尽管使用冷冻组织进行了全基因组 DNA 甲基化分析以进行精确诊断,但肿瘤细胞的比例不足,仅观察到正常小脑。然后,我们使用福尔马林固定石蜡包埋切片进行了全面的基因分析,结果显示 MYCN 扩增而 IDH1、IDH2 或组蛋白 H3 没有改变。最终,该患者被诊断为小儿型弥漫性高级别神经胶质瘤,H3 野生型和 IDH 野生型。总之,对于小儿脑肿瘤病例应考虑进行全面的遗传和表观遗传分析。