Department of Dermatology, Thomas Jefferson University, Philadelphia, Pennsylvania.
Department of Dermatology, Thomas Jefferson University, Philadelphia, Pennsylvania.
J Am Acad Dermatol. 2024 Jul;91(1):1-10. doi: 10.1016/j.jaad.2023.08.020. Epub 2023 Aug 17.
Paraneoplastic pemphigus/paraneoplastic autoimmune multiorgan syndrome (PNP/PAMS) is a highly fatal autoimmune blistering disease. The condition occurs in patients with underlying benign or malignant neoplasms, most commonly lymphoproliferative disorders. Both humoral and cell-mediated immunities contribute to the pathogenesis, and autoantibodies against plakin family proteins are characteristic. Patients typically present with severe stomatitis and polymorphous skin lesions, which are often resistant to treatment. Bronchiolitis obliterans (BO) is a frequent complication which contributes to the high mortality rate of PNP/PAMS. Given the rarity of this disorder and heterogeneity of clinical presentation, clinicians should maintain a high index of suspicion for PNP/PAMS to avoid delayed diagnosis. In this first part of a two-part continuing medical education (CME) series, risk factors, pathogenesis, and clinical features of PNP/PAMS are discussed.
副肿瘤天疱疮/副肿瘤自身免疫性多器官综合征(PNP/PAMS)是一种高致命性的自身免疫性水疱病。这种疾病发生在有潜在良性或恶性肿瘤的患者中,最常见的是淋巴增生性疾病。体液和细胞免疫都有助于发病机制,自身抗体针对桥粒蛋白家族蛋白是特征性的。患者通常表现为严重的口炎和多形性皮肤损伤,这些损伤往往对治疗有抗性。细支气管闭塞(BO)是一种常见的并发症,导致 PNP/PAMS 的高死亡率。鉴于这种疾病的罕见性和临床表现的异质性,临床医生应保持对 PNP/PAMS 的高度怀疑,以避免延迟诊断。在这个 CME 系列的两部分中的第一部分中,讨论了 PNP/PAMS 的危险因素、发病机制和临床特征。