Cancer and Blood Disorders Institute, Johns Hopkins All Children's Hospital, St Petersburg, FL.
Center for Cancer and Blood Disorders.
Pediatrics. 2024 Jan 1;153(2). doi: 10.1542/peds.2023-062643.
Sickle cell disease (SCD) is a chronic hematologic disorder which causes progressive cerebral arteriopathy beginning in childhood. As a result, arterial ischemic stroke is a major cause of morbidity and mortality in SCD, and SCD is a leading cause of childhood stroke worldwide. Allogenic hematopoietic stem cell transplant (HSCT) may be curative for individuals with SCD. Long-term outcomes and effects are currently being studied. In this report, we describe a child with SCD who presented with arterial ischemic stroke at 6 years of age and was found to have a severe form of cerebral large vessel arteriopathy by catheter-directed angiography. The patient initially underwent revascularization surgery by indirect superficial temporal artery to middle cerebral artery bypass, and 1 year later, he underwent curative HSCT. Approximately 3 years after HSCT, repeat catheter-directed angiography revealed a striking reversal of cerebral large vessel arteriopathy. This article reveals a previously unrecognized and potentially beneficial effect of HSCT that may ameliorate cerebral large vessel arteriopathy and improve cerebrovascular health for children with SCD.
镰状细胞病(SCD)是一种慢性血液病,可导致儿童时期开始进行性脑血管病。因此,动脉缺血性卒中是 SCD 患者发病率和死亡率的主要原因,SCD 也是全球儿童卒中的主要原因。同种异体造血干细胞移植(HSCT)可能对 SCD 患者具有治愈作用。目前正在研究其长期结果和影响。在本报告中,我们描述了一名患有 SCD 的儿童,他在 6 岁时出现动脉缺血性卒中,并通过导管定向血管造影发现严重的大脑大血管动脉病。患者最初接受了间接颞浅动脉到大脑中动脉旁路的血运重建手术,1 年后接受了治愈性 HSCT。HSCT 后约 3 年,重复导管定向血管造影显示大脑大血管动脉病明显逆转。本文揭示了 HSCT 的一个以前未被认识到的潜在有益作用,可能改善 SCD 儿童的大脑大血管动脉病和改善脑血管健康。