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17q12重复综合征的复杂神经精神表现:一例报告。

Complex neuropsychiatric presentation of 17q12 duplication syndrome: A case report.

作者信息

Das Soumitra, Samarasinghe Lochana, Deva Sheryl, Fernandez Co Elaiza Marie, Poudel Sujan, Dave Tirth, Prasad Sakshi, Sarangi Ashish

机构信息

Department of Psychiatry, Western Health, Footscray, VIC, Australia.

Base Hospital Nikaweratiya, Nikaweratiya, Srilanka.

出版信息

SAGE Open Med Case Rep. 2024 Feb 19;12:2050313X241233184. doi: 10.1177/2050313X241233184. eCollection 2024.

Abstract

The chromosomal band 17q12 is characterized by a high density of genes and is bordered by segmental duplications, the structural arrangement of which increases the susceptibility of the region to deletions and duplications. Duplication of 17q12 is a rare genetic condition associated with variable characteristics from clinically asymptomatic to intellectual disabilities, seizures, and behavioral problems. The variability in phenotype is primarily due to variable expressivity and incomplete penetrance. Diagnosis is mostly established by chromosomal microarray. Treatment involves a multidisciplinary approach. We present a case of a 43-year-old female who initially presented with hyperphagia and was eventually diagnosed with bulimia nervosa, anxiety, mood disorder, and personality disorder. Additional research is required to better understand the impact of 17q12 duplication syndrome on the development of bulimia nervosa since its pathogenesis has not been adequately described in the current literature.

摘要

染色体带17q12的特点是基因密度高,且由节段性重复序列界定,其结构排列增加了该区域发生缺失和重复的易感性。17q12重复是一种罕见的遗传疾病,其相关特征各异,从临床无症状到智力残疾、癫痫和行为问题不等。表型的变异性主要归因于可变表达和不完全外显率。诊断大多通过染色体微阵列确定。治疗采用多学科方法。我们报告一例43岁女性病例,该患者最初表现为食欲亢进,最终被诊断为神经性贪食症、焦虑症、情绪障碍和人格障碍。由于目前文献中尚未充分描述其发病机制,因此需要进一步研究以更好地了解17q12重复综合征对神经性贪食症发展的影响。

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本文引用的文献

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Rev Paul Pediatr. 2023 Jan 20;41:e2021387. doi: 10.1590/1984-0462/2023/41/2021387. eCollection 2023.
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