Oushy Soliman, Orbach Darren B
Department of Neurosurgery, Boston Children's Hospital, Harvard Medical School, Boston, Massachusetts, USA.
Department of Neurosurgery, Mayo Clinic, Rochester, Minnesota, USA.
J Neurointerv Surg. 2025 Jan 17;17(2):200-204. doi: 10.1136/jnis-2023-021355.
Infantile-type dural arteriovenous shunts (IDAVS) are rare and heterogeneous vascular lesions, complicating their classification and management. The current tripartite classification of pediatric dural arteriovenous shunts (DAVS) into dural sinus malformation, infantile-type, and adult-type, does not stand up to scrutiny, given the variable presentations of the latter two types in children. We estimate the prevalence of IDAVS and evaluate the long term outcomes after endovascular treatment (EVT).
A retrospective review of a pediatric cerebrovascular database between 2006 and 2023 was conducted. Clinical and radiographic data were analyzed to evaluate the presentation and long term outcomes of IDAVS.
IDAVS were identified in 8 (0.5%) of 1463 patients, with mean age at diagnosis of 34.7 months; male infants comprised 62.5%. The most common clinical presentations included macrocephaly (37.5%), seizures (25%), and dilated scalp veins (25%). EVT was performed in 87.5% of cases, averaging 5.8 procedures per patient. Radiographic obliteration was observed in 28.6%. Good clinical outcomes (modified Rankin Scale score of ≤2) were achieved in 85.7%. Our findings showcased discrepancies and limitations in the current classification of pediatric DAVS, prompting a re-evaluation.
IDAVS accounted for a small proportion of pediatric cerebrovascular pathologies, with markedly heterogeneous presentations. Stepwise selective embolization was associated with favorable outcomes, and is recommended over an aggressive approach with the goal of complete angiographic obliteration. Our proposed revised classification system bifurcates pediatric DAVS into dural sinus malformations and all other DAVS that are manifest in children, thereby enhancing diagnostic clarity and therapeutic approaches.
婴儿型硬脑膜动静脉分流(IDAVS)是罕见且异质性的血管病变,这使其分类和管理变得复杂。目前将小儿硬脑膜动静脉分流(DAVS)分为硬脑膜窦畸形、婴儿型和成人型的三方分类法,鉴于后两种类型在儿童中的表现多变,经不起仔细推敲。我们估计了IDAVS的患病率,并评估了血管内治疗(EVT)后的长期结局。
对2006年至2023年的小儿脑血管数据库进行回顾性研究。分析临床和影像学数据,以评估IDAVS的表现和长期结局。
在1463例患者中有8例(0.5%)被诊断为IDAVS,诊断时的平均年龄为34.7个月;男婴占62.5%。最常见的临床表现包括巨头畸形(37.5%)、癫痫发作(25%)和头皮静脉扩张(25%)。87.5%的病例接受了EVT,平均每位患者进行5.8次手术。观察到28.6%的病例在影像学上达到闭塞。85.7%的患者获得了良好的临床结局(改良Rankin量表评分为≤2)。我们的研究结果显示了目前小儿DAVS分类中的差异和局限性,促使重新评估。
IDAVS在小儿脑血管病变中占比小,表现明显异质。逐步选择性栓塞与良好结局相关,建议采用这种方法,而不是以血管造影完全闭塞为目标的激进方法。我们提出的修订分类系统将小儿DAVS分为硬脑膜窦畸形和在儿童中表现出的所有其他DAVS,从而提高诊断清晰度和治疗方法。