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韩国莱伯遗传性视神经病变患者的线粒体 DNA 突变。

Mitochondrial DNA mutations in Korean patients with Leber's hereditary optic neuropathy.

机构信息

Department of Ophthalmology, Seoul National University College of Medicine, Seoul National University Bundang Hospital, 82 Gumi-ro, 173 Beon-gil, Bundang-gu, Seongnam, Gyeonggi-do, 13620, Republic of Korea.

Department of Laboratory Medicine, Seoul National University College of Medicine, Seoul National University Hospital, Seoul, Republic of Korea.

出版信息

Sci Rep. 2024 Mar 8;14(1):5702. doi: 10.1038/s41598-024-56215-x.

Abstract

In order to explore the spectrum of mitochondrial DNA (mtDNA) mutations in Korean patients with Leber's hereditary optic neuropathy (LHON), we investigated the spectrum of mtDNA mutations in 145 Korean probands confirmed with the diagnosis of LHON. Total genomic DNA was isolated from the peripheral blood leukocytes of the patients with suspected LHON, and mtDNA mutations were identified by direct sequencing. Analysis of mtDNA mutations revealed seven primary LHON mutations including the nucleotide positions (nps) 11778A (101 probands, 69.2%), 14484C (31 probands, 21.2%), 3460A (5 probands, 3.4%), and G3635A, G3733A, C4171A, and G13051A mutations in one proband each. In addition, two provisional mtDNA mutations at nps T3472C, and G13259A were each found in one proband, respectively. Another provisional mtDNA mutation at np T3394C was found in two probands. In conclusion, the spectrum of mtDNA mutations in Korean patients with LHON may differ from other ethnicities, which is characterized by high prevalence of 11778A and 14484C mutations, and a low prevalence of the 3460A mutation.

摘要

为了探究韩国莱伯遗传性视神经病变(LHON)患者中线粒体 DNA(mtDNA)突变的频谱,我们对 145 名经 LHON 确诊的韩国先证者的 mtDNA 突变谱进行了研究。从疑似 LHON 患者的外周血白细胞中提取总基因组 DNA,并通过直接测序鉴定 mtDNA 突变。mtDNA 突变分析显示,包括核苷酸位置(nps)11778A(101 名先证者,占 69.2%)、14484C(31 名先证者,占 21.2%)、3460A(5 名先证者,占 3.4%)和 G3635A、G3733A、C4171A 和 G13051A 突变在内的七种主要 LHON 突变,以及 nps T3472C 和 G13259A 各一个的两种暂定 mtDNA 突变,以及 np T3394C 两个暂定 mtDNA 突变,分别在一个先证者中发现。总之,韩国 LHON 患者 mtDNA 突变谱可能与其他种族不同,其特点是 11778A 和 14484C 突变的高发生率,以及 3460A 突变的低发生率。

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