Noor Fadila, Ogunleye Olushola O, Rahim Hussan, Cluzet Valerie
Internal Medicine, Vassar Brothers Medical Center/Nuvance Health, Poughkeepsie, USA.
Infectious Diseases, Vassar Brothers Medical Center/Nuvance Health, Poughkeepsie, USA.
Cureus. 2024 Apr 14;16(4):e58259. doi: 10.7759/cureus.58259. eCollection 2024 Apr.
Cryoglobulinemia may result in small-to-medium vessel vasculitis. Central nervous system (CNS) involvement is rare, and presentation may range from stroke/transient ischemic attack, reversible ischemic neurological deficits, to encephalopathic syndromes. This is a rare case discussing cryoglobulinemia with CNS involvement. A 56-year-old female with a history of cryoglobulinemia was found unresponsive to verbal and physical stimuli. She was admitted to the intensive care unit. CT head without contrast showed diffuse cerebral edema and mass effect in the right cerebral hemisphere causing right to left midline shift, brainstem infarct, hemorrhage in the right lateral ventricle, and obstruction of the fourth ventricle. The patient was managed with hypertonic saline, external ventricular drain (EVD) placement, and high-dose steroids, which led to an improvement in her condition. In conclusion, testing for cryoglobulins and serologic tests for hepatitis C should be considered in syndromes of cerebral ischemia or infarction without an obvious cause, especially in young individuals since encephalopathy may be reversible. Cryoglobulinemia with CNS manifestations may be associated with purpura, high RF, and low C4. The treatment can be a combination of steroids, immunosuppressants, plasmapheresis, and rituximab. Cyclophosphamide may also be considered as adjunctive therapy to corticosteroids in rapidly progressive severe neurological complications. Further research for treatment standards in nonviral cryoglobulinemia is needed.
冷球蛋白血症可能导致中小血管血管炎。中枢神经系统(CNS)受累较为罕见,表现形式可从卒中/短暂性脑缺血发作、可逆性缺血性神经功能缺损到脑病综合征。这是一例讨论冷球蛋白血症合并中枢神经系统受累的罕见病例。一名有冷球蛋白血症病史的56岁女性被发现对言语和身体刺激无反应。她被收入重症监护病房。头颅非增强CT显示弥漫性脑水肿,右侧大脑半球有占位效应,导致中线从右向左移位、脑干梗死、右侧侧脑室出血以及第四脑室梗阻。该患者接受了高渗盐水治疗、外置脑室引流(EVD)置管以及大剂量类固醇治疗,病情有所改善。总之,对于无明显病因的脑缺血或梗死综合征,尤其是年轻个体,应考虑检测冷球蛋白和进行丙型肝炎血清学检测,因为脑病可能是可逆的。伴有中枢神经系统表现的冷球蛋白血症可能与紫癜高类风湿因子(RF)和低补体C4有关。治疗可采用类固醇、免疫抑制剂、血浆置换和利妥昔单抗联合。在快速进展的严重神经并发症中,环磷酰胺也可考虑作为皮质类固醇的辅助治疗。需要对非病毒性冷球蛋白血症的治疗标准进行进一步研究。