Department of Speech and Hearing Sciences, University College Cork, Ireland.
Department of Music, University College Cork, Ireland.
Am J Speech Lang Pathol. 2024 Jul 3;33(4):2002-2022. doi: 10.1044/2024_AJSLP-23-00375. Epub 2024 Jun 11.
Few studies have explored the feasibility of online language interventions for young children with Down syndrome. Additionally, none have manipulated dose frequency or reported on the use of music as a medium through which language and sign can be learned.
The purpose of this study was to (a) examine the feasibility and acceptability of an online language through music intervention for young children (1-3;6 years) with Down syndrome and (b) compare effectiveness at two intervention dose frequencies.
The study was carried out in two phases using a mixed-methods design. Qualitative data were gathered from parents to examine feasibility when implementing a video-based language intervention. Seventy-six families participated in an online language intervention at home. Effectiveness was examined comparing two groups, randomly assigned to a high and low dose frequency. The Down Syndrome Education (DSE) checklists (combined) were the primary outcome measure. Process data were gathered to determine intervention acceptability in practice and to identify factors that would improve successful future implementation. Acceptability data were analyzed with reference to the theoretical framework of acceptability (Version 2).
Forty-three parents completed the Phase 1 scoping questionnaire, five of whom took part in focus groups. Once weekly morning sessions were indicated as the preferred scheduling choice. Phase 2 quantitative data were analyzed using beta regression adjusted for baseline scores and indicated no additional benefit to receiving the higher dose. However, exploratory interaction models suggested that the efficacy of the high-dose intervention was higher (than low-dose intervention) in participants with higher baseline DSE performance. Parents perceived the intervention to be effective and positive for the family.
The results add to our knowledge of real-world effective online interventions and suggest that a critical minimum language level is required for children with Down syndrome to benefit optimally from a higher intervention dose frequency.
很少有研究探索针对唐氏综合征儿童的在线语言干预的可行性。此外,没有研究操纵剂量频率或报告使用音乐作为学习语言和手语的媒介。
本研究的目的是:(a) 检验针对唐氏综合征幼儿(1-3 岁;6 岁)的在线音乐语言干预的可行性和可接受性;(b) 比较两种干预剂量频率的效果。
该研究采用混合方法设计分两个阶段进行。通过父母收集定性数据,以考察实施基于视频的语言干预的可行性。76 个家庭在家中参与了在线语言干预。通过比较随机分配到高剂量和低剂量频率的两个组来检验有效性。唐氏综合征教育(DSE)检查表(合并)是主要的结果测量。收集过程数据以确定干预在实践中的可接受性,并确定改善未来成功实施的因素。参考可接受性理论框架(第 2 版)分析可接受性数据。
43 位家长完成了第 1 阶段范围界定问卷,其中 5 位家长参加了焦点小组。每周一早上的会议被认为是首选的日程安排。使用贝塔回归对基线分数进行调整后,对第 2 阶段的定量数据进行了分析,结果表明,接受更高剂量的干预并没有额外的益处。然而,探索性交互模型表明,对于基线 DSE 表现较高的参与者,高剂量干预的效果(比低剂量干预)更高。家长认为干预对家庭有效且积极。
研究结果增加了我们对现实世界有效在线干预的了解,并表明唐氏综合征儿童需要有一个关键的最低语言水平,才能从更高的干预剂量频率中获得最佳效果。