You Axel, Lippens Léa S, Fayet Odessa-Maud, Maillard Solène, Betemps Laureline, Grondin Antony, Vilquin Jean-Thomas, Dragin Nadine, Le Panse Rozen
Sorbonne University, Institut National de la Santé et de la Recherche Médicale (INSERM), Association Institute of Myology, Center of Research in Myology, UMRS 974, Paris, France.
Front Immunol. 2025 Mar 31;16:1521382. doi: 10.3389/fimmu.2025.1521382. eCollection 2025.
Myasthenia gravis (MG) is an autoimmune disorder primarily caused by autoantibodies that target the acetylcholine receptor (AChR) at the neuromuscular junction (NMJ). The classical experimental autoimmune myasthenia gravis (C-EAMG) mouse model has long been used by immunizing mice with acetylcholine receptor from Torpedo fish (T-AChR), combined with complete Freund's adjuvant (CFA). This mixture is administered via subcutaneous injections into the hind footpads and back, but CFA often causes strong inflammatory reactions, including lesions at the injection sites. Our objective was to develop a new EAMG model (N-EAMG) that is more compliant with animal welfare. C57Bl/6 mice were immunized twice weekly by intraperitoneal (i.p.) injection of T-AChR with a poly(I:C) and lipopolysaccharide (LPS) adjuvant mix. Control mice were injected with either physiological saline or the adjuvant mix alone. Various doses and injection schedules were tested, and the new model was compared with C-EAMG. Clinical symptoms were scored, antibody subtypes against T-AChR and mouse AChR were measured, and NMJ morphology and functionality were evaluated. We demonstrate that the N-EAMG model is at least as effective as the C-EAMG model. Moreover, similar to the C-EAMG model, the N-EAMG model is characterized by the production of T-AChR and m-AChR antibodies. This model also exhibited alterations in transmission at the NMJ due to antibody attack, resulting in a decrease in AChR surface area and increased AChR fragmentation. Symptoms were similar in both models but appeared more rapidly in the N-EAMG model. In addition, investigating the sensitization mechanism, we showed that i.p. injections of T-AChR with the poly(I:C)/LPS adjuvant mix, led to the recruitment in monocytes and changes in the two peritoneal macrophage subpopulations that were able to phagocytose T-AChR. These observations suggest that macrophage subtypes, albeit with varying efficiency, present the T-AChR to immune cells, leading to a specific immune response and the development of anti-AChR antibodies. In conclusion, our results demonstrate that this novel EAMG model is as effective as the C-EAMG model and offers several advantages. In particular, this model is more suitable for animal welfare and can replace the classical model in preclinical and fundamental research.
重症肌无力(MG)是一种自身免疫性疾病,主要由靶向神经肌肉接头(NMJ)处乙酰胆碱受体(AChR)的自身抗体引起。经典的实验性自身免疫性重症肌无力(C-EAMG)小鼠模型长期以来一直通过用来自电鳐的乙酰胆碱受体(T-AChR)免疫小鼠,并结合完全弗氏佐剂(CFA)来构建。这种混合物通过皮下注射到后足垫和背部,但CFA常常会引起强烈的炎症反应,包括注射部位的损伤。我们的目标是开发一种更符合动物福利的新型EAMG模型(N-EAMG)。通过每周两次腹腔内(i.p.)注射T-AChR与聚肌胞苷酸(poly(I:C))和脂多糖(LPS)佐剂混合物来免疫C57Bl/6小鼠。对照小鼠注射生理盐水或仅注射佐剂混合物。测试了各种剂量和注射方案,并将新模型与C-EAMG进行比较。对临床症状进行评分,测量针对T-AChR和小鼠AChR的抗体亚型,并评估NMJ的形态和功能。我们证明N-EAMG模型至少与C-EAMG模型一样有效。此外,与C-EAMG模型类似,N-EAMG模型的特征是产生T-AChR和m-AChR抗体。由于抗体攻击,该模型在NMJ处的传递也出现改变,导致AChR表面积减少和AChR碎片化增加。两种模型的症状相似,但在N-EAMG模型中出现得更快。此外,在研究致敏机制时,我们发现腹腔内注射T-AChR与poly(I:C)/LPS佐剂混合物会导致单核细胞募集以及两种能够吞噬T-AChR的腹膜巨噬细胞亚群发生变化。这些观察结果表明,巨噬细胞亚型尽管效率不同,但会将T-AChR呈递给免疫细胞,从而引发特异性免疫反应并产生抗AChR抗体。总之,我们的结果表明这种新型EAMG模型与C-EAMG模型一样有效,并具有多个优点。特别是,该模型更适合动物福利,可在临床前和基础研究中替代经典模型。