Rigante Donato, Manna Raffaele, Candelli Marcello
Department of Life Sciences and Public Health, Fondazione Policlinico Universitario A. Gemelli IRCCS, Largo A. Gemelli 8, 00168, Rome, Italy.
Università Cattolica Sacro Cuore, Rome, Italy.
Intern Emerg Med. 2025 Jun 13. doi: 10.1007/s11739-025-03999-z.
The underlying mechanisms responsible for the periodic fever, aphthous stomatitis, pharyngitis, and cervical adenitis (PFAPA) syndrome are unknown. The main purpose of this study was to retrospectively assess different characteristics and lab-work investigations including serum 25(OH)-vitamin D levels in patients with PFAPA syndrome evaluated at our University hospital during the decade 2014-2024. The medical charts of 151 children with diagnosis of PFAPA syndrome were retrospectively evaluated: for each patient demographic data, clinical manifestations during acute episodes, and laboratory analyses during a well-being phase within the trimester following PFAPA diagnosis were examined. A focus was given to serum 25-hydroxyvitamin D [25(OH)-vitamin D] concentration, recognized as the functional status indicator for vitamin D. Based on the reference values for normal serum 25(OH)-vitamin D, patients were divided into two groups (inadequate versus normal vitamin D levels); the groups were compared to identify if hypovitaminosis D could have any relationship with the evolution of PFAPA syndrome over time. Forty-five PFAPA patients (30% of the whole cohort) had serum 25(OH)-vitamin D below the normal reference (< 30 ng/mL), and inadequate vitamin D serum levels were associated with a persistent pattern of PFAPA syndrome, also showing an inverse correlation with age at disease onset. This study offers a static snapshot of vitamin D status in children with PFAPA syndrome, without accounting for specific time points, and suggests that serum 25(OH)-vitamin D levels might contribute to a longer duration of the recurring PFAPA symptoms.
周期性发热、口疮性口炎、咽炎和颈淋巴结炎(PFAPA)综合征的潜在发病机制尚不清楚。本研究的主要目的是回顾性评估2014年至2024年期间在我们大学医院接受评估的PFAPA综合征患者的不同特征和实验室检查,包括血清25(OH)-维生素D水平。对151例诊断为PFAPA综合征的儿童病历进行回顾性评估:检查每位患者的人口统计学数据、急性发作期的临床表现以及PFAPA诊断后三个月内健康期的实验室分析。重点关注血清25-羟基维生素D[25(OH)-维生素D]浓度,其被认为是维生素D的功能状态指标。根据正常血清25(OH)-维生素D的参考值,将患者分为两组(维生素D水平不足组与正常组);比较两组以确定维生素D缺乏是否与PFAPA综合征随时间的演变有任何关系。45例PFAPA患者(占整个队列的30%)血清25(OH)-维生素D低于正常参考值(<30 ng/mL),维生素D血清水平不足与PFAPA综合征的持续模式相关,也与疾病发病年龄呈负相关。本研究提供了PFAPA综合征患儿维生素D状态的静态快照,未考虑特定时间点,并表明血清25(OH)-维生素D水平可能导致PFAPA复发症状持续时间更长。