Malami A B, Ogbozor B E, Okolo C C, Aborisade A O, Mahmud U B, Abulfathi A A, Adeyemo Y I
Department of Child Dental Health, Bayero University, Kano, Kano State, Nigeria.
Department of Child Dental Health, Aminu Kano Teaching Hospital, Kano, Kano State, Nigeria.
Case Rep Dent. 2025 Sep 16;2025:5519222. doi: 10.1155/crid/5519222. eCollection 2025.
Oligodontia represents the developmental absence of six or more teeth, posing significant challenges for masticatory function, speech, and psychosocial well-being. While extensively documented in developed countries, limited reports exist from resource-constrained settings in Africa. This study presents two pediatric cases of oligodontia managed with available resources and analyzes their clinical presentations against current literature. This case report was prepared following the CARE guidelines to ensure methodological rigor and completeness. Case 1, a 10-year-old female with a history of missing anterior teeth from birth, with no associated systemic abnormalities and no contributory family history, but with deranged alkaline phosphatase. To address masticatory function, speech, and esthetic problems, removable partial dentures were fabricated for both jaws. Case 2, a 10-year-old female with a family history of congenitally missing teeth but no other features of syndromic oligodontia, with an associated crown fracture involving the enamel, dentine, and pulp of the maxillary right central incisor, peg-shaped maxillary right lateral incisor, and retained mandibular central incisors. Systemic features of mild acanthosis nigricans, nail abnormalities, and hypohidrosis were observed with deranged alkaline phosphatase. To restore speech and masticatory function, root canal treatment and postretained crown restoration of the maxillary right central incisor and composite resin restoration for the peg-shaped maxillary right lateral incisors and retained lower central incisor teeth were done. Early diagnosis and multidisciplinary management of oligodontia significantly improve functional outcomes and quality of life. Resource limitations necessitated adaptive treatment approaches while maintaining therapeutic efficacy.
少牙症表现为六个或更多牙齿先天性缺失,给咀嚼功能、言语及心理社会健康带来重大挑战。虽然在发达国家已有广泛记载,但非洲资源有限地区的相关报道较少。本研究介绍了两例利用现有资源治疗的小儿少牙症病例,并对照当前文献分析了其临床表现。本病例报告是按照CARE指南编写的,以确保方法的严谨性和完整性。病例1为一名10岁女性,自出生起就有前牙缺失史,无相关全身异常,家族史无明显影响因素,但碱性磷酸酶紊乱。为解决咀嚼功能、言语及美观问题,为上下颌制作了可摘局部义齿。病例2为一名10岁女性,有先天性缺牙家族史,但无综合征性少牙症的其他特征,伴有上颌右中切牙、上颌右侧切牙呈钉状及下颌中切牙滞留的牙冠骨折,累及釉质、牙本质和牙髓。观察到有轻度黑棘皮病、指甲异常和少汗等全身特征,碱性磷酸酶紊乱。为恢复言语和咀嚼功能,对上颌右中切牙进行了根管治疗和桩冠修复,对上颌右钉状侧切牙和滞留的下颌中切牙进行了复合树脂修复。少牙症的早期诊断和多学科管理可显著改善功能结局和生活质量。尽管资源有限,但在保持治疗效果的同时仍需采取适应性治疗方法。