Bujdoso G, Lenz W
Eur J Pediatr. 1980 May;133(3):207-15. doi: 10.1007/BF00496078.
Monodactyly is a sign of at least 3 different types of autosomal dominant ectrodactyly. In the first type only the 1st and the 5th or only the 5th toes are present on both feet. The trait is fully expressed in all affected children of patients. No skipping of a generation has been observed. Both parents of several affected children may be normal, or one parent may show minor manifestations only. Single strand mutation is suggested as an explanation of these exceptional cases. Monodactyly is seen less frequently in the second type, ectrodactyly, ectodermal dysplasia and cleft lip and palate (the EEC syndrome), than in the first type. The limb defects are more variable. The third type of ectrodactyly shows extreme intrafamilial variability, comprising various degrees of ectrodactyly, monodactyly and adactyly, defects of the ulna and/or of the tibia. Minor manifestations often occur in affected children of patients. Skipping of a generation is not uncommon.
单指(趾)畸形是至少3种不同类型常染色体显性缺指(趾)畸形的一种体征。在第一种类型中,双足仅存在第1和第5趾,或者仅存在第5趾。该性状在患者所有受影响的子女中均充分表达。未观察到隔代遗传现象。几个受影响子女的双亲可能均正常,或者一方可能仅表现出轻微症状。单链突变被认为是这些特殊情况的一种解释。与第一种类型相比,单指(趾)畸形在第二种类型即缺指(趾)、外胚层发育不良和唇腭裂(EEC综合征)中较少见。肢体缺陷更具变异性。第三种类型的缺指(趾)畸形表现出极大的家族内变异性,包括不同程度的缺指(趾)、单指(趾)和无指(趾)畸形,以及尺骨和/或胫骨缺陷。在患者受影响的子女中常出现轻微症状。隔代遗传并不罕见。