Heutink P, Zguricas J, van Oosterhout L, Breedveld G J, Testers L, Sandkuijl L A, Snijders P J, Weissenbach J, Lindhout D, Hovius S E
Department of Clinical Genetics, Erasmus University, Rotterdam, The Netherlands.
Nat Genet. 1994 Mar;6(3):287-92. doi: 10.1038/ng0394-287.
Triphalangeal thumb is a developmental anomaly, sometimes dominantly transmitted, characterized by a long, finger-like thumb with three phalanges instead of two. The underlying genetic defect is unknown, but presumably involves genes that regulate the differentiation of the developing forelimb. In two large kindreds with triphalangeal thumb, evidence for linkage to the long arm of chromosome 7 was obtained with a maximum lod score of 12.61. Multipoint linkage and haplotype analysis placed the gene close to the telomere of the long arm. To our knowledge this is the first time that a human gene involved solely in the pathologic morphogenesis of the hand and feet has been localized.
三节指骨拇指是一种发育异常,有时为显性遗传,其特征是拇指长且呈手指状,有三节指骨而非正常的两节。潜在的基因缺陷尚不清楚,但推测涉及调控发育中前肢分化的基因。在两个患有三节指骨拇指的大家族中,获得了与7号染色体长臂连锁的证据,最大对数优势分数为12.61。多点连锁和单倍型分析将该基因定位于长臂的端粒附近。据我们所知,这是首次定位一个仅涉及手足病理形态发生过程的人类基因。