Gullino E, Abrate M, Zerbino E, Bricchi G, Rattazzi P D
Department of Genetics, Hospital USSL 61, Savigliano (Cuneo), Italy.
Prenat Diagn. 1993 May;13(5):411-6. doi: 10.1002/pd.1970130514.
A prenatal diagnosis of arthrogryposis multiplex congenita (AMC) has been carried out on a 19-week-old fetus by means of echography. The ultrasonographic characteristics were unnatural position of the four limbs associated with articular anomalies together with absence of active fetal movements. A therapeutic interruption of pregnancy was performed and the diagnosis was confirmed. At autopsy, architectural disorder of the motor neurons of the anterior medullary horn revealed a neuropathic pathogenesis of the arthrogryposis. Moreover, at the lumbar level the spinal cord was progressively replaced by heterotopic bony tissue which caused a more severe deformity of the lower limbs compared with the upper. The aspects of anatomo-pathological, genetic, and differential diagnosis are discussed showing the precocity of the prenatal diagnosis and the peculiarity of the aetiology of our case.
通过超声检查对一名19周大的胎儿进行了先天性多发性关节挛缩症(AMC)的产前诊断。超声特征为四肢位置异常并伴有关节畸形,同时胎儿无主动活动。进行了治疗性引产,诊断得到证实。尸检显示,延髓前角运动神经元的结构紊乱揭示了关节挛缩症的神经病变发病机制。此外,在腰椎水平,脊髓逐渐被异位骨组织替代,与上肢相比,这导致下肢出现更严重的畸形。本文讨论了解剖病理学、遗传学及鉴别诊断方面的情况,展示了产前诊断的早熟性以及本病例病因的特殊性。