Haeusler G, Guchev Z, Köhler I, Schober E, Haas O, Frisch H
Pediatric Department, University of Vienna, Austria.
Klin Padiatr. 1993 Sep-Oct;205(5):351-3. doi: 10.1055/s-2007-1025247.
Two boys are presented with the clinical features of cerebral gigantism and chromosomal variants which have not been described so far in this syndrome. In the first boy a de novo pericentric inversion of chromosome Y was found, the karyotypes of all other investigated family members were normal. The patient had an obstructive hypertrophic cardiomyopathy and atrial septal defect type II. The second boy had inherited pericentric inversion of the heterochromatic region of chromosome 9 from his mother. This chromosome 9 variant was also found in his sister who had a similar phenotype but without gigantism. Endocrine evaluation demonstrated normal results in both boys. The intellectual achievement in both cases was average.
两名男孩表现出脑性巨人症的临床特征以及该综合征迄今尚未描述过的染色体变异。在第一个男孩中发现了Y染色体的新发臂间倒位,所有其他被调查家庭成员的核型均正常。该患者患有梗阻性肥厚型心肌病和II型房间隔缺损。第二个男孩从他母亲那里遗传了9号染色体异染色质区的臂间倒位。在他患有相似表型但无巨人症的妹妹身上也发现了这种9号染色体变异。两名男孩的内分泌评估结果均正常。两例患者的智力发育水平均为中等。