Ford A M, Pombo-de-Oliveira M S, McCarthy K P, MacLean J M, Carrico K C, Vincent R F, Greaves M
Leukaemia Research Fund Centre, Institute for Cancer Research, London, UK.
Blood. 1997 Jan 1;89(1):281-5.
Acute leukemia has a high concordance rate in young identical twins and in infants this is known, from molecular analysis, to reflect an in utero origin in one twin followed by prenatal metastasis to the other twin via intraplacental anastomoses. The situation in older twins with leukemia has been less clear. We describe a pair of identical twins who were diagnosed with a T-cell malignancy at 9 and 11 years of age, one with T-cell non-Hodgkin's lymphoma and the other with T-cell acute lymphoblastic leukemia. Leukemic cells from the twins shared the same TCR beta gene rearrangement with an identical 11 bp N region. The most plausible interpretation of this result is that these malignancies were initiated in one twin fetus in utero, in a single T-lineage cell that had stable bi-allelic TCR beta rearrangements. Progeny of this cell then spread to the other twin before birth via shared placental vasculature. This was then followed by a 9- and 11-year preleukemic latent period before clinical disease manifestation as leukemia or lymphoma. This result has considerable implications for the etiology and natural history of pediatric leukemia.
急性白血病在年轻同卵双胞胎中的一致性率很高,对于婴儿,从分子分析可知,这反映了白血病起源于一个胎儿的子宫内,随后通过胎盘内吻合术在产前转移至另一个胎儿。年龄较大的白血病双胞胎的情况尚不清楚。我们描述了一对同卵双胞胎,他们分别在9岁和11岁时被诊断患有T细胞恶性肿瘤,一个患有T细胞非霍奇金淋巴瘤,另一个患有T细胞急性淋巴细胞白血病。双胞胎的白血病细胞具有相同的TCRβ基因重排以及相同的11bp N区域。对此结果最合理的解释是,这些恶性肿瘤起源于子宫内一个胎儿的单个T系细胞,该细胞具有稳定的双等位基因TCRβ重排。该细胞的后代随后在出生前通过共享的胎盘血管系统扩散到另一个胎儿。随后在临床出现白血病或淋巴瘤之前有9年和11年的白血病前期潜伏期。这一结果对儿童白血病的病因和自然史具有重要意义。