Sigaudy S, Toutain A, Moncla A, Fredouille C, Bourlière B, Ayme S, Philip N
Department of Medical Genetics and Foetopathology, Hôpital d'Enfants de la Timone, Marseilles, France.
Am J Med Genet. 1998 Oct 30;80(1):16-24.
Microcephalic and osteodysplastic primordial dwarfism (MODP) types I, II, and III were defined by Majewski et al. in 1982. This group of syndromes was characterized by intrauterine growth retardation, microcephaly, and typical facial appearance with prominent nose and micrognathia. Type II was clearly different, both clinically and radiologically, whereas types I and III shared manifestations. Distinction between the latter two was established on the basis of subtle radiological differences. In 1967, Taybi and Linder described another syndrome with microcephalic congenital dwarfism. There is a consensus that MODP type I and III and Taybi-Linder cephaloskeletal dysplasia represent the same disorder. We report on four patients with MODP type Taybi-Linder syndromes, two of whom were born to unrelated but consanguineous parents, while the other two were sibs. Second-trimester prenatal detection by ultrasonography was possible in one case. Consanguinity in two cases and recurrence among sibs are consistent with autosomal recessive inheritance.
小头畸形和骨发育不良性原始侏儒症(MODP)I型、II型和III型由马耶夫斯基等人于1982年定义。这组综合征的特征为宫内生长迟缓、小头畸形以及典型的面部外观,伴有突出的鼻子和小颌畸形。II型在临床和放射学上明显不同,而I型和III型有共同的表现。后两者之间的区别是基于细微的放射学差异确定的。1967年,泰比和林德描述了另一种伴有小头畸形先天性侏儒症的综合征。目前已达成共识,MODP I型和III型以及泰比-林德头骨骼发育异常代表同一种疾病。我们报告了4例泰比-林德综合征MODP患者,其中2例患者的父母无亲缘关系但为近亲结婚,另外2例为同胞。其中1例在孕中期通过超声检查得以产前诊断。2例存在近亲结婚以及同胞中出现复发情况符合常染色体隐性遗传。