Dupond J L, Gil H, Bouhaddi M, Magy N, Berthier S, Regnard J
Department of Internal Medicine, University Hospital, Besançon, France.
Clin Exp Rheumatol. 1999 Nov-Dec;17(6):733-6.
Acute dysautonomia is a disorder characterized by severe sympathetic and parasympathetic failure with relative preservation of motor and sensory function. The disease is considered to be idiopathic in most cases, but there is now a trend towards considering the disorder as an uncommon variant of Guillain Barré syndrome. We report two cases of acute dysautonomia which did not fulfill the criteria of the idiopathic form. The first case was associated with Sjögren's syndrome and the second with thyroiditis and antiganglioside antibodies which were correlated with the severity of the disease. Intravenous gammaglobulin (IVGG) was effective in both cases, as has been reported for the idiopathic form, and in one case the treatment was associated with an increase in the supine and standing plasma norepinephrine levels, thus substantiating the positive effects of IVGG on the orthostatic blood pressure and heart rate. We conclude that the spectrum of acute dysautonomia is superimposable on that of the inflammatory peripheric neuropathies and should include both the idiopathic form and dysautonomia with autoimmune associated disorders. IVGG are effective and seems to act by increasing plasma norepinephrine levels.
急性自主神经功能障碍是一种以严重的交感神经和副交感神经功能衰竭为特征,而运动和感觉功能相对保留的疾病。在大多数情况下,该疾病被认为是特发性的,但现在有一种趋势是将这种疾病视为吉兰-巴雷综合征的一种罕见变体。我们报告了两例不符合特发性形式标准的急性自主神经功能障碍病例。第一例与干燥综合征有关,第二例与甲状腺炎及抗神经节苷脂抗体有关,这些抗体与疾病的严重程度相关。静脉注射免疫球蛋白(IVGG)在这两例中均有效,正如特发性形式的报道那样,在其中一例中,治疗与仰卧位和站立位血浆去甲肾上腺素水平升高有关,从而证实了IVGG对直立性血压和心率的积极作用。我们得出结论,急性自主神经功能障碍的范围与炎症性周围神经病的范围重叠,应包括特发性形式和伴有自身免疫相关疾病的自主神经功能障碍。IVGG是有效的,似乎是通过提高血浆去甲肾上腺素水平起作用。