Ito E, Kitazawa J, Arai K, Otomo H, Endo Y, Imashuku S, Yokoyama M
Department of Pediatrics, Hirosaki University School of Medicine, Japan.
Int J Hematol. 2000 Apr;71(3):263-5.
We report a case of Epstein-Barr virus (EBV)-associated hemophagocytic lymphohistiocytosis (HLH) with clonal karyotype abnormality. A 5-year-old boy was admitted to our hospital with persistent high-grade fever, hepatomegaly, and pancytopenia. Laboratory data disclosed a coagulation abnormality and severe liver damage. Clonal proliferation of EBV-infected cells was detected in the bone marrow by Southern hybridization, and bone marrow cells exhibited clonal chromosomal abnormality. Although the patient was treated with immunochemotherapy according to the HLH94 protocol, the disease recurred during the induction therapy, and the patient died of disseminated intravascular coagulopathy. Considering this aggressive and fatal clinical course, it is important to take intensive therapeutic measures if karyotype abnormality is noted in the treatment of EBV-HLH patients.
我们报告一例伴有克隆性核型异常的爱泼斯坦-巴尔病毒(EBV)相关噬血细胞性淋巴组织细胞增生症(HLH)。一名5岁男孩因持续高热、肝肿大和全血细胞减少入住我院。实验室检查发现凝血异常和严重肝损伤。通过Southern杂交在骨髓中检测到EBV感染细胞的克隆性增殖,骨髓细胞表现出克隆性染色体异常。尽管该患者按照HLH94方案接受了免疫化疗,但在诱导治疗期间疾病复发,患者死于弥散性血管内凝血。考虑到这种侵袭性和致命的临床病程,在治疗EBV-HLH患者时,如果发现核型异常,采取强化治疗措施很重要。