Perlman M, Benady S, Saggi E
Pediatrics. 1979 Feb;63(2):238-41.
The serious prognostic implications of familial dysautonomia (FD) for the affected individual and his family make early definitive diagnosis mandatory. Familial dysautonomia has rarely been diagnosed in the neonatal period in hitherto unaffected families. We describe here three such newborn patients to reinforce the limited data available on this subject. In spite of the variability of expression and the incompleteness of the manifestations of FD in the neonatal period, as well as the presence of a number of "dysautonomic" features in normal newborns, we believe that it is possible to establish a diagnosis of FD neonatally. We pay particular note to the altered state of consciousness and behavior in neonatal FD, the unusual posture and limb movements, and the swallowing disorder with tendency to neonatal aspiration. In addition, the incidental finding of bile pigment in the amniotic fluid of an affected fetus without hemolytic disease may hint at a possible approach to fetal diagnosis of this condition.
家族性自主神经功能障碍(FD)对患者及其家庭具有严重的预后影响,因此早期明确诊断至关重要。在迄今未受影响的家庭中,新生儿期很少诊断出家族性自主神经功能障碍。我们在此描述三例此类新生儿患者,以充实关于该主题的有限数据。尽管FD在新生儿期的表现存在变异性且表现不完全,以及正常新生儿中存在一些“自主神经功能障碍”特征,但我们认为在新生儿期有可能诊断出FD。我们特别注意新生儿FD中意识和行为状态的改变、异常姿势和肢体运动,以及伴有新生儿误吸倾向的吞咽障碍。此外,在无溶血性疾病的受影响胎儿羊水中偶然发现胆汁色素,可能提示对此疾病进行胎儿诊断的一种可能方法。