Dhillon H, Ge Y, Minter R M, Prima V, Moldawer L L, Muzyczka N, Zolotukhin S, Kalra P S, Kalra S P
Department of Physiology, University of Florida Brain Institute, College of Medicine, 32610, Gainesville, FL, USA.
Regul Pept. 2000 Aug 25;92(1-3):97-105. doi: 10.1016/s0167-0115(00)00155-5.
We investigated the long-term effects of physiological levels of leptin produced by gene therapy on body weight (BW) and expression of genes that encode orexigenic and anorexigenic peptides in the hypothalamus. Recombinant adeno-associated viral vector (rAAV), a non-pathogenic and non-immunogenic vector, encoding leptin (betaOb) was generated and administered iv to ob/ob mice lacking endogenous leptin. Whereas the lowest dose of rAAV-betaOb (6x10(9) particles) was ineffective, the middle dose (6x10(10) particles) curbed BW gain without affecting food consumption for 75 days of observation. A ten-fold higher dose (6x10(11) particles) resulted in increased blood leptin levels and suppressed both BW gain and food consumption throughout the duration of the experiment. rAAV-betaOb doses that either curbed BW without affecting food consumption or evoked BW loss and reduced food intake, decreased the expression of genes encoding the orexigenic peptides, neuropeptide Y and agouti-related peptide in the ARC, and the two doses were equally effective. Concomitantly, the expression of genes encoding the anorexigenic peptide, alpha-melanocyte stimulating hormone and cocaine-and-amphetamine regulatory transcript, was augmented with the latter gene displaying a dose-dependant response. These results document the efficacy of delivering biologically active leptin for extended periods by an iv injection of rAAV-betaOb and show that physiological leptin concentrations simultaneously exert a tonic inhibitory effect on orexigenic and a stimulatory effect on anorexigenic signaling in the hypothalamus. This intricate dynamic interplay induced by leptin regulates BW with or without an effect on food intake in leptin-deficient ob/ob mice. Further, these results suggest that gene therapy is an effective mode of delivery to the hypothalamus of those therapeutic proteins that cross the blood-brain barrier to ameliorate neuroendocrine disorders.
我们研究了基因疗法产生的生理水平瘦素对体重(BW)以及下丘脑内编码促食欲和抑食欲肽的基因表达的长期影响。构建了一种编码瘦素(βOb)的重组腺相关病毒载体(rAAV),该载体无致病性且无免疫原性,并通过静脉注射给予缺乏内源性瘦素的ob/ob小鼠。最低剂量的rAAV-βOb(6×10⁹个颗粒)无效,中等剂量(6×10¹⁰个颗粒)在75天的观察期内抑制了体重增加且不影响食物消耗。剂量高10倍(6×10¹¹个颗粒)导致血液瘦素水平升高,并在整个实验期间抑制了体重增加和食物消耗。抑制体重增加而不影响食物消耗或引起体重减轻并减少食物摄入量的rAAV-βOb剂量,降低了弓状核中编码促食欲肽神经肽Y和刺鼠相关肽的基因表达,且这两种剂量效果相同。同时,编码抑食欲肽α-黑素细胞刺激素和可卡因-安非他明调节转录物的基因表达增加,后者的基因呈现剂量依赖性反应。这些结果证明了通过静脉注射rAAV-βOb长时间递送生物活性瘦素的有效性,并表明生理瘦素浓度同时对下丘脑的促食欲信号发挥强直性抑制作用,对抑食欲信号发挥刺激作用。瘦素诱导的这种复杂动态相互作用在瘦素缺乏的ob/ob小鼠中调节体重,无论是否影响食物摄入。此外,这些结果表明基因疗法是将那些能够穿过血脑屏障以改善神经内分泌紊乱的治疗性蛋白质递送至下丘脑的有效方式。