Quinzii C, Castellani C
Cystic Fibrosis Center, Azienda Ospedaliera, Verona, Italy.
J Endocrinol Invest. 2000 Nov;23(10):684-9. doi: 10.1007/BF03343794.
Congenital bilateral absence of the vas deferens (CBAVD) is a relatively frequent cause of male infertility accounting for 1-2% of cases of male sterility and at least 6% of cases of obstructive azoospermia. In the last decade a genetic basis for CBAVD has been provided by its association with cystic fibrosis (CF) and nowadays CBAVD is in most cases considered to be a mild or incomplete form of CF disease. Many individuals with CBAVD show usually mild CF-compatible clinical manifestations, but the long-term prognosis could possibly not be as innocuous as it presently looks: more data will be available through medium or long-term follow-up studies. Once a correct diagnosis of CBAVD has been formulated and if the couple is planning a pregnancy by artificial reproductive technology, it is crucial to test both the affected male and his partner for CFTR mutations. Such testing has a number of complex implications and should always be performed together with genetic counselling. Other issues are debated in this article including CF mutations in non-CBAVD forms of male infertility, and the potentially misleading role of CF genetic analysis when used to rule out other possible causes of infertility in azoospermic men.
先天性双侧输精管缺如(CBAVD)是男性不育相对常见的原因,占男性不育病例的1%-2%,至少占梗阻性无精子症病例的6%。在过去十年中,CBAVD与囊性纤维化(CF)的关联为其提供了遗传基础,如今在大多数情况下,CBAVD被认为是CF疾病的一种轻度或不完全形式。许多患有CBAVD的个体通常表现出与CF相符的轻度临床表现,但长期预后可能不像目前看起来那么无害:通过中长期随访研究将可获得更多数据。一旦对CBAVD做出正确诊断,并且如果这对夫妇计划通过辅助生殖技术怀孕,对受影响的男性及其伴侣进行CFTR突变检测至关重要。这种检测有许多复杂的影响,并且应该始终与遗传咨询一起进行。本文还讨论了其他问题,包括非CBAVD形式的男性不育中的CF突变,以及CF基因分析在用于排除无精子症男性其他可能的不育原因时可能产生的误导作用。