Verrijn Stuart A A, Huisman M, van Straaten H L, Bakker J C, Arabin B
Department of Neonatology, Isala Klinieken Zwolle, The Netherlands.
J Perinat Med. 2000;28(6):497-501. doi: 10.1515/JPM.2000.067.
Myotonic dystrophy is a multi-organ disease inherited in a complicated way. Congenital myotonic dystrophy is a distinct entity with severe symptoms leading to a high rate of perinatal morbidity and mortality. The occurrence of congenital myotonic dystrophy often allows a subsequent diagnosis in the mother with important implications for her life, her further pregnancies and offspring. Genetic principles of anticipation and somatic mosaicism are involved and hamper the prenatal diagnostic possibilities. A family is presented in which maternal myotonic dystrophy and congenital myotonic dystrophy were diagnosed after the third pregnancy. The key features leading to the diagnosis were obstetric history, neonatal hypotonia and asphyxia, facial abnormalities in the mother together with the inability to bury eyelashes and delayed release of grip after shaking hands. The disorder is reviewed with respect to clinical symptoms, pathogenesis and genetics.
强直性肌营养不良是一种以复杂方式遗传的多器官疾病。先天性强直性肌营养不良是一种独特的疾病实体,症状严重,导致围产期发病率和死亡率很高。先天性强直性肌营养不良的发生常常使得能够对母亲进行后续诊断,这对她的生活、进一步怀孕和后代都有重要影响。其中涉及到遗传的早现和体细胞镶嵌现象等遗传原理,这阻碍了产前诊断的可能性。本文介绍了一个家庭,该家庭中母亲的强直性肌营养不良和先天性强直性肌营养不良是在第三次怀孕后才被诊断出来的。导致诊断的关键特征包括产科病史、新生儿肌张力减退和窒息、母亲面部异常,以及无法埋住睫毛和握手后抓握松开延迟。本文就该疾病的临床症状、发病机制和遗传学进行了综述。