Watanabe Y, Sato M, Tokui K, Yukumi S, Koga S, Nezu K, Matsui H, Murakami H, Kawachi K
Second Department of Surgery, Ehime University, Shigenobu 791-0295, Japan.
Surg Endosc. 2000 Jun;14(6):595. doi: 10.1007/s004640000095. Epub 2000 Apr 25.
Blue rubber bleb nevus syndrome is characterized by gastrointestinal and cutaneous hemangiomas and gastrointestinal bleeding causing anemia. We report a unique case of this syndrome in an adult woman. It was associated with congenital heart disease, for which the patient underwent surgery at 12 months of age, and cutaneous hemangiomas, for which surgery was performed later in childhood. Gastrointestinal bleeding was diagnosed and treated when she was 21 years of age after a workup for iron deficiency anemia. Successful total resection of all gastrointestinal hemangiomas was performed by minimally invasive surgery with gastric, small intestinal, and colonic fiberscopy and laparoscopy. The postoperative course was uneventful. The patient could walk the day after surgery, and she was discharged from the hospital 14 days after surgery. Our experience and findings given in other reports suggest that total resection of hemangiomas should be the final goal and that minimal skin incision is preferable for this benign disease, with multiendoscope-assisted treatment to ensure that any hemangiomas remaining in the gastrointestinal tract are not overlooked.
蓝色橡皮疱痣综合征的特征是胃肠道和皮肤血管瘤以及导致贫血的胃肠道出血。我们报告了一名成年女性患此综合征的独特病例。该病例与先天性心脏病相关,患者12个月大时接受了心脏手术,还患有皮肤血管瘤,童年后期进行了手术。21岁时,在对缺铁性贫血进行检查后诊断并治疗了胃肠道出血。通过胃、小肠和结肠纤维内镜检查及腹腔镜进行微创手术,成功地完全切除了所有胃肠道血管瘤。术后过程顺利。患者术后第二天即可行走,术后14天出院。我们的经验以及其他报告中的发现表明,血管瘤的完全切除应是最终目标,对于这种良性疾病,应尽可能减少皮肤切口,并采用多内镜辅助治疗,以确保不遗漏任何残留于胃肠道的血管瘤。