Benedetto B, Madden R, Kurbanov A, Braden G, Freeman J, Lipkowitz G S
Departments of Surgery, Transplant Division, Medicine, Renal Division, and Pathology, Baystate Medical Center, Springfield, MA, USA.
Am J Kidney Dis. 2001 May;37(5):E37. doi: 10.1016/s0272-6386(05)90001-2.
Adenine phosphoribosyltransferase (APRT) deficiency is a rarely diagnosed cause of renal allograft dysfunction. We report the case of a 42-year-old man who presented in 1996 with idiopathic renal failure. Native kidney biopsy showed extensive microcrystalline interstitial nephritis. The patient subsequently underwent a living-related kidney transplant with excellent early graft function. During the next year, however, he had worsening allograft function, and allograft biopsy showed recurrent interstitial nephritis. Further chemical and spectroscopic analysis showed this lesion to be an annular microcrystalline nephritis consistent with APRT deficiency. This diagnosis was confirmed on erythrocyte assay. Treatment with allopurinol and a low-purine diet led to improvement and stabilization of renal function. APRT is a rare cause of renal allograft dysfunction requiring a high index of suspicion for early diagnosis and treatment. Increased physician awareness in the United States may hasten diagnosis and limit the morbidity associated with this disease.
腺嘌呤磷酸核糖转移酶(APRT)缺乏症是肾移植功能障碍的一种罕见诊断病因。我们报告一例42岁男性病例,该患者于1996年出现特发性肾衰竭。自体肾活检显示广泛的微晶间质性肾炎。该患者随后接受了亲属活体肾移植,早期移植肾功能良好。然而,在接下来的一年里,他的移植肾功能逐渐恶化,移植肾活检显示复发性间质性肾炎。进一步的化学和光谱分析表明,该病变为与APRT缺乏症相符的环状微晶性肾炎。红细胞检测证实了这一诊断。使用别嘌醇和低嘌呤饮食治疗后,肾功能得到改善并稳定。APRT缺乏症是肾移植功能障碍的罕见病因,需要高度怀疑以进行早期诊断和治疗。美国医生意识的提高可能会加快诊断并限制与该疾病相关的发病率。