Kemkemer Ralf, Schrank Stephanie, Vogel Walther, Gruler Hans, Kaufmann Dieter
Department of Biophysics, University of Ulm, Albert Einstein Allee 11, D-89070 Ulm, Germany.
Proc Natl Acad Sci U S A. 2002 Oct 15;99(21):13783-8. doi: 10.1073/pnas.212386999. Epub 2002 Oct 4.
In human diseases related to tumor-suppressor genes, it is suggested that only the complete loss of the protein results in specific symptoms such as tumor formation, whereas simple reduction of protein quantity to 50%, called haploinsufficiency, essentially does not affect cellular behavior. Using a model of gene expression, it was presumed that haploinsufficiency is related to an increased noise in gene expression also in vivo [Cook, D. L., Gerber, A. N. & Tapscott, S. J. (1998) Proc. Natl. Acad. Sci. USA 95, 15641-15646]. Here, we demonstrate that haploinsufficiency of the tumor-suppressor gene neurofibromatosis type 1 (NF1) results in an increased variation of dendrite formation in cultured NF1 melanocytes. These morphological differences between NF1 and control melanocytes can be described by a mathematical model in which the cell is considered to be a self-organized automaton. The model describes the adjustment of the cells to a set point and includes a noise term that allows for stochastic processes. It describes the experimental data of control and NF1 melanocytes. In the cells haploinsufficient for NF1 we found an altered signal-to-noise ratio detectable as increased variation in dendrite formation in two of three investigated morphological parameters. We also suggest that in vivo NF1 haploinsufficiency results in an increased noise in cellular regulation and that this effect of haploinsufficiency may be found also in other tumor suppressors.
在与肿瘤抑制基因相关的人类疾病中,有人提出只有蛋白质的完全缺失才会导致特定症状,如肿瘤形成,而蛋白质数量简单减少至50%(称为单倍剂量不足)基本上不会影响细胞行为。利用基因表达模型推测,单倍剂量不足在体内也与基因表达噪声增加有关[库克,D. L.,格伯,A. N. & 塔普斯科特,S. J.(1998年)《美国国家科学院院刊》95,15641 - 15646]。在此,我们证明肿瘤抑制基因1型神经纤维瘤病(NF1)的单倍剂量不足会导致培养的NF1黑色素细胞中树突形成的变化增加。NF1黑色素细胞与对照黑色素细胞之间的这些形态差异可以用一个数学模型来描述,该模型将细胞视为一个自组织自动机。该模型描述了细胞对设定点的调节,并包括一个允许随机过程的噪声项。它描述了对照和NF1黑色素细胞的实验数据。在NF1单倍剂量不足的细胞中,我们发现在三个研究的形态学参数中的两个参数中,树突形成的变化增加可检测到信噪比改变。我们还提出,在体内NF1单倍剂量不足会导致细胞调节中的噪声增加,并且这种单倍剂量不足的效应可能在其他肿瘤抑制因子中也能发现。