Haenggeli Christine, Kato Ann C
Department of Pharmacology (APSIC) and Division of Clinical Neuromuscular Research, Faculty of Medicine, University of Geneva, 1 rue Michel-Servet, 1211 Geneva 4, Switzerland.
Neurosci Lett. 2002 Dec 19;335(1):39-43. doi: 10.1016/s0304-3940(02)01140-0.
Amyotrophic lateral sclerosis (ALS) is characterized by the progressive degeneration of selective motoneuron populations, yet it remains unclear why some groups of motoneurons are more vulnerable than others. Our aim was to compare the motoneuron loss in five cranial nuclei at different stages of the disease in three mouse models of ALS: two naturally occurring murine models (progressive motor neuronopathy (pmn) and wobbler) and a transgenic mouse model with a human G93A mutation in the superoxide dismutase-1 (SOD1) gene. By quantifying these different motoneuron populations we report that the degree of degeneration in the various cranial motoneuron nuclei depends on the mouse model and the stage of the disease. The biologically most significant difference between the mutations occurs in the oculomotor/trochlear nucleus which is affected in the pmn mouse but not in the wobbler and SOD G93A mice. These results suggest that there is a selective degeneration of cranial motoneurons in these mouse models as in ALS patients.
肌萎缩侧索硬化症(ALS)的特征是选择性运动神经元群体的进行性退化,但尚不清楚为何某些运动神经元组比其他组更易受损。我们的目的是在三种ALS小鼠模型中比较疾病不同阶段五个颅神经核中的运动神经元损失:两种自然发生的小鼠模型(进行性运动神经元病(pmn)和摇摆症)以及一种在超氧化物歧化酶-1(SOD1)基因中具有人类G93A突变的转基因小鼠模型。通过对这些不同的运动神经元群体进行定量分析,我们报告称,各个颅运动神经核的退化程度取决于小鼠模型和疾病阶段。突变之间生物学上最显著的差异发生在动眼神经/滑车神经核,该核在pmn小鼠中受到影响,但在摇摆症小鼠和SOD G93A小鼠中未受影响。这些结果表明,与ALS患者一样,这些小鼠模型中存在颅运动神经元的选择性退化。