Porter Rebecca M, Lane E Birgitte
Cancer Research UK Cell Structure Research Group, School of Life Sciences, MSI/WTB Complex, University of Dundee, Dundee DD1 5EH, UK.
Trends Genet. 2003 May;19(5):278-85. doi: 10.1016/s0168-9525(03)00071-4.
A large number of mutations in keratin genes underlie inherited tissue fragility disorders of epithelia. The genotype-phenotype correlations emerging from these studies provide a rich source of information about the function of keratins that would have taken decades to achieve by a purely transgenic approach. Human disease studies are being supplemented by engineered mouse mutant studies, which give access to the effects of genetic alterations unlikely to occur naturally. Evidence is emerging that the great diversity of keratins might be required to enable cells to adapt their structure in response to different signalling pathways.
角蛋白基因的大量突变是上皮遗传性组织脆性疾病的基础。这些研究中出现的基因型-表型相关性为角蛋白功能提供了丰富的信息来源,而这通过纯粹的转基因方法可能需要数十年才能实现。人类疾病研究正通过工程小鼠突变体研究得到补充,后者能够探究不太可能自然发生的基因改变的影响。越来越多的证据表明,可能需要角蛋白的巨大多样性才能使细胞根据不同的信号通路调整其结构。