Mukherjee Monisha, Chaturvedi L S, Srivastava Sandhya, Mittal R D, Mittal Balraj
Department of Medical Genetics, Sanjay Gandhi Postgraduate Institute of Medical Sciences, Raebareli Road, Lucknow 226014, India.
Exp Mol Med. 2003 Apr 30;35(2):113-7. doi: 10.1038/emm.2003.16.
Dinucleotide repeat polymorphism based genetic analysis is a powerful approach to gain insight into rare genetic events like germline mosaicism and de novo mutations. The loss of heterozygosity of polymorphic dinucleotide loci at "deletional hotspot" of dystrophin gene can provide direct evidence of carrier status in female relatives of affected DMD patients with overlapped exonic deletions. We have used 4 STR loci of the central deletional hotspot of the dystrophin gene for genetic analysis in sporadic unrelated DMD families. Twenty-nine mothers of sporadic deletional cases were analysed and their carrier status was determined. Eighteen of them showed heterozygosity in the deleted loci suggesting the occurrence of de novo mutations. In 9 cases, the carrier status was indeterminate while 2 showed germline mosaicism. Our observations reiterated the importance of STR analysis in determining the status of mothers of sporadic deletional DMD cases in order to provide proper genetic counselling.
基于二核苷酸重复多态性的基因分析是深入了解种系嵌合体和新发突变等罕见遗传事件的有力方法。在肌营养不良蛋白基因“缺失热点”处多态性二核苷酸位点的杂合性丧失可为患有重叠外显子缺失的DMD患者女性亲属的携带者状态提供直接证据。我们使用了肌营养不良蛋白基因中央缺失热点的4个STR位点对散发性无关DMD家系进行基因分析。对29例散发性缺失病例的母亲进行了分析,并确定了她们的携带者状态。其中18例在缺失位点显示杂合性,提示发生了新发突变。9例携带者状态无法确定,2例显示种系嵌合体。我们的观察结果再次强调了STR分析在确定散发性缺失DMD病例母亲状态以提供适当遗传咨询方面的重要性。