Wohlfart Sabine, Sebinger David, Gruber Petra, Buch Judith, Polgar Doris, Krupitza Georg, Rosner Margit, Hengstschläger Markus, Raderer Markus, Chott Andreas, Müllauer Leonhard
Department of Pathology, University of Vienna, General Hospital Vienna, Vienna, Austria.
Am J Pathol. 2004 Mar;164(3):1081-9. doi: 10.1016/S0002-9440(10)63195-1.
A loss of FAS (CD95) function has been proposed to constitute an important step in early mucosa-associated lymphoid tissue (MALT) lymphoma development and FAS mutations have been recognized in malignant lymphomas, in particular at extranodal sites. Since primary gastric lymphomas frequently exhibit resistance to FAS-mediated apoptosis, we investigated whether FAS is mutated in 18 gastric MALT lymphomas and 28 diffuse large B-cell lymphomas (DLBCL). We detected seven mutations in five lymphomas, one MALT lymphoma and four DLBCL; two DLBCL had two mutations. The MALT lymphoma exhibited a point mutation in the splice donor region of intron 3. Three DLBCL had missense mutations in exon 2, which encodes a signal peptide and a portion of the extracellular FAS ligand-binding domain. One DLBCL carried a point mutation in the splice donor region of intron 8, which would result in exon skipping. Two DLBCL harbored a missense mutation in exon 9, which encodes the intracellular death domain. The two death domain mutations inhibited FAS ligand-induced apoptosis in a dominant-negative mode, when transiently expressed in human T47D breast carcinoma and Jurkat T cells. A signal peptide and an extracellular domain mutation, however, failed to inhibit apoptosis in these transfection assays. They are likely to reduce apoptosis in lymphoma cells solely by a loss of function. In summary, our data show that FAS mutations are rare in primary gastric MALT lymphomas (5.6%) but occur in a subset of primary gastric DLBCL (14.3%) and suggest that these mutations contribute to the pathogenesis of gastric lymphomas by rendering lymphocytes resistant to apoptosis.
FAS(CD95)功能丧失被认为是早期黏膜相关淋巴组织(MALT)淋巴瘤发展的重要步骤,并且FAS突变在恶性淋巴瘤中已得到确认,尤其是在结外部位。由于原发性胃淋巴瘤经常表现出对FAS介导的凋亡的抗性,我们研究了18例胃MALT淋巴瘤和28例弥漫性大B细胞淋巴瘤(DLBCL)中FAS是否发生突变。我们在5例淋巴瘤中检测到7个突变,其中1例MALT淋巴瘤和4例DLBCL;2例DLBCL有两个突变。该MALT淋巴瘤在第3内含子的剪接供体区域出现点突变。3例DLBCL在第2外显子中有错义突变,该外显子编码信号肽和细胞外FAS配体结合域的一部分。1例DLBCL在第8内含子的剪接供体区域发生点突变,这将导致外显子跳跃。2例DLBCL在第9外显子中有错义突变,该外显子编码细胞内死亡结构域。当在人T47D乳腺癌细胞和Jurkat T细胞中瞬时表达时,这两个死亡结构域突变以显性负性模式抑制FAS配体诱导的凋亡。然而,在这些转染实验中,一个信号肽和一个细胞外结构域突变未能抑制凋亡。它们可能仅通过功能丧失来减少淋巴瘤细胞中的凋亡。总之,我们的数据表明FAS突变在原发性胃MALT淋巴瘤中很少见(5.6%),但在原发性胃DLBCL的一个亚组中出现(14.3%),并表明这些突变通过使淋巴细胞对凋亡产生抗性而有助于胃淋巴瘤的发病机制。