Smith Rachel Lynne, Sundberg Joyce, Shamiyah Eli, Dyer Alan, Pachman Lauren M
Department of Pediatrics, Division of Immunology/ Rheumatology, Northwestern University Feinberg School of Medicine, Chicago, Illinois, USA.
J Rheumatol. 2004 Aug;31(8):1644-9.
To determine associations of dermatological findings in children with juvenile dermatomyositis (JDM) with specific nailfold capillary (NFC) structural abnormalities.
Sixty newly diagnosed, previously untreated children who met the Bohan-Peter criteria for definite JDM were seen between 1993 and 2002. They were classified by duration of untreated disease and by a disease activity score (DAS) composed of separate subscores for dermatological (DAS skin) and musculoskeletal (DAS muscle) findings. Routine NFC measurements yielded the number of end row loops, arboreal (bushy), and dilated capillary loops. Laboratory testing included muscle enzymes, von Willebrand Factor Antigen, and neopterin.
DAS skin, but not DAS muscle, was associated with NFC end row capillary loss (rs = -0.394, p = 0.008). End row capillary loss (reflecting avascularity), arboreal (bushy), and dilated capillary loops (reflecting change in vascular morphology) were each associated with longer untreated symptom duration (rs = -0.401, rs = 0.534, rs = 0.371).
End row capillary loss measured by NFC was associated with the dermatological, but not musculoskeletal manifestations of JDM, suggesting that damage to skin and muscle may each have distinct disease pathophysiology. In JDM, skin involvement indicates a vasculopathy that progresses with increasing duration of untreated disease and is not revealed by standard serological laboratory tests. We propose that the cutaneous manifestations of JDM are associated with vascular disease and warrant aggressive therapy.
确定青少年皮肌炎(JDM)患儿的皮肤表现与特定甲襞毛细血管(NFC)结构异常之间的关联。
1993年至2002年间,对60名新诊断、未经治疗且符合博汉-彼得明确JDM标准的儿童进行了观察。根据未治疗疾病的持续时间以及由皮肤(DAS皮肤)和肌肉骨骼(DAS肌肉)表现的单独子评分组成的疾病活动评分(DAS)对他们进行分类。常规NFC测量得出终末排襻、树枝状(浓密)和扩张毛细血管襻的数量。实验室检测包括肌肉酶、血管性血友病因子抗原和新蝶呤。
DAS皮肤而非DAS肌肉与NFC终末排毛细血管缺失相关(rs = -0.394,p = 0.008)。终末排毛细血管缺失(反映无血管状态)、树枝状(浓密)和扩张毛细血管襻(反映血管形态变化)均与未治疗症状持续时间较长相关(rs = -0.401,rs = 0.534,rs = 0.371)。
通过NFC测量的终末排毛细血管缺失与JDM的皮肤表现相关,但与肌肉骨骼表现无关,这表明皮肤和肌肉损伤可能各自具有不同的疾病病理生理学。在JDM中,皮肤受累表明存在一种血管病变,其随着未治疗疾病持续时间的增加而进展,并且标准血清学实验室检测未显示出来。我们提出JDM的皮肤表现与血管疾病相关,需要积极治疗。