Finlay M, Laperriere N, Bristow R G
Department of Radiation Oncology, Princess Margaret Hospital (University Health Network) and University of Toronto, Toronto, Ontario, Canada.
Clin Oncol (R Coll Radiol). 2005 Feb;17(1):54-6. doi: 10.1016/j.clon.2004.06.028.
Marfan syndrome (MFS) is a heritable disorder of the connective tissue which has been linked to mutations in the FBN (fibrillin-1) gene. Murine knockouts of the FBN gene show increased interstitial fibrosis and TGF-beta (tumor growth factor-beta) gene activation. Abnormal TGF-beta expression has previously been linked to radiation-induced fibrosis, suggesting a possible link between MFS and increased late effects following radiotherapy. Herein we report two cases in which MFS patients treated with radical radiotherapy without undue acute or late radiotherapy toxicity suggesting that radiotherapy should not be withheld from MFS patients. MFS patients may provide a unique clinico-translational setting to test associations between FBN mutations, TGF-beta activation and the risk of tissue fibrosis.
马凡综合征(MFS)是一种遗传性结缔组织疾病,与原纤维蛋白-1(FBN)基因突变有关。FBN基因敲除的小鼠表现出间质纤维化增加和转化生长因子-β(TGF-β)基因激活。先前已发现异常的TGF-β表达与放射性纤维化有关,这表明MFS与放疗后晚期效应增加之间可能存在联系。在此,我们报告两例接受根治性放疗的MFS患者,未出现过度的急性或晚期放疗毒性,这表明不应拒绝为MFS患者进行放疗。MFS患者可能提供一个独特的临床转化环境,以测试FBN突变、TGF-β激活与组织纤维化风险之间的关联。