Prasad Priyajit, Salem Ronald R, Mangla Rakhee, Aslanian Harry, Jain Dhanpat, Lee Jeffrey
Department of Internal Medicine, Yale University School of Medicine, New Haven, Connecticut 06510, USA.
Yale J Biol Med. 2004 Sep;77(5-6):143-8.
Autoimmune pancreatitis is a rare but important cause of pancreatitis that is becoming increasingly recognized in the West. Lymphoplasmacytic sclerosing pancreatitis (LPSP) is a benign form of chronic pancreatitis characterized clinically by infrequent attacks of abdominal pain, jaundice, and weight loss, and pathologically by focal or diffuse chronic or lymphoplasmacytic inflammatory infiltrates centered around pancreatic ducts and ductules, accompanied by obliterative phlebitis, acinar atrophy, and interstitial fibrosis. It has been described alone or as a part of the spectrum of autoimmune gallbladder and biliary tract disease, with clinical, radiological, and pathological overlap reported with primary sclerosing cholangitis. It has been described as "primary sclerosing pancreatitis," "sclerosing cholangitis," "non-alcoholic duct destructive chronic pancreatitis," and "autoimmune pancreatitis." We report a case of LPSP that mimicked pancreatic adenocarcinoma and was subsequently treated with a pylorus-preserving Whipple procedure. This may point towards a primary biliary autoimmune process involving the pancreatic duct, causing a benign form of chronic pancreatitis that may be difficult to characterize pre-operatively to avoid surgery. This case typifies the growing awareness of this relatively recently characterized clinical entity, its similar presentation to pancreatic carcinoma, and the importance for LPSP to be included in the differential diagnosis of pancreaticobiliary disease. Finally, we review the literature.
自身免疫性胰腺炎是一种罕见但重要的胰腺炎病因,在西方正越来越受到认可。淋巴细胞浆细胞性硬化性胰腺炎(LPSP)是一种慢性胰腺炎的良性形式,临床上以腹痛发作不频繁、黄疸和体重减轻为特征,病理上以围绕胰管和小导管的局灶性或弥漫性慢性或淋巴细胞浆细胞性炎性浸润为特征,伴有闭塞性静脉炎、腺泡萎缩和间质纤维化。它曾被单独描述,或作为自身免疫性胆囊和胆道疾病谱的一部分,有报道称其在临床、放射学和病理学上与原发性硬化性胆管炎有重叠。它曾被描述为“原发性硬化性胰腺炎”“硬化性胆管炎”“非酒精性导管破坏性慢性胰腺炎”和“自身免疫性胰腺炎”。我们报告一例LPSP病例,其临床表现酷似胰腺腺癌,随后接受了保留幽门的胰十二指肠切除术。这可能提示存在一种涉及胰管的原发性胆汁自身免疫过程,导致一种良性慢性胰腺炎,术前可能难以明确诊断以避免手术。该病例体现了对这种相对较新发现的临床实体的认识不断增加,其与胰腺癌的相似表现,以及将LPSP纳入胰胆疾病鉴别诊断的重要性。最后,我们对相关文献进行了综述。