Edwards Paul C, McVaney Tim
Oral and Maxillofacial Pathology, Department of General Dentistry, Creighton University School of Dentistry, Omaha, NE 68178, USA.
Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2005 Nov;100(5):585-91. doi: 10.1016/j.tripleo.2005.02.069.
Hereditary hemorrhagic telangiectasia (HHT) is an inherited syndrome characterized by mucocutaneous telangiectases that commonly involve the tongue, lips, fingers, and conjunctiva. While root resorption has been reported in association with central hemangiomas of bone, the association of HHT with external cervical root resorption has not been described to date. We report a case of a 57-year-old female with HTT who presented with advanced cervical root resorption involving multiple maxillary anterior teeth. Histologic examination of the gingival tissue adjacent to the area of root resorption demonstrated multiple thin-walled vascular elements as well as larger vascular channels surrounded by a thickened muscular layer. We hypothesize that the external root resorption seen in this case is the result of the HHT-related vascular process in the adjacent gingival tissue.
遗传性出血性毛细血管扩张症(HHT)是一种遗传性综合征,其特征为黏膜皮肤毛细血管扩张,常见于舌头、嘴唇、手指和结膜。虽然已有报道牙根吸收与骨中心血管瘤有关,但HHT与颈外牙根吸收的关联迄今尚未见描述。我们报告一例57岁患有HHT的女性,其出现累及多颗上颌前牙的晚期颈外牙根吸收。对牙根吸收区域相邻的牙龈组织进行组织学检查,发现多个薄壁血管成分以及被增厚肌层包围的较大血管通道。我们推测该病例中所见的牙根外吸收是相邻牙龈组织中与HHT相关的血管病变所致。