Hays Arthur P, Naini Ali, He Cui Zhen, Mitsumoto Hiroshi, Rowland Lewis P
Department of Pathology (Neuropathology), Columbia University Medical Center, PH15th Stem, Room 124, 630 West 168th Street, New York, NY 10032, USA.
J Neurol Sci. 2006 Mar 15;242(1-2):67-9. doi: 10.1016/j.jns.2005.11.016. Epub 2006 Jan 19.
Autopsy of patients with sporadic amyotrophic lateral sclerosis (ALS) rarely provides clues to a genetic etiology. We studied a 66-year-old woman who developed progressive weakness, fasciculations and upper motor neuron signs 1 year after mastectomy and chemotherapy for a breast carcinoma. She died 14 months after the onset of neurological symptoms. Autopsy showed characteristic features of ALS but also with posterior column degeneration and conglomerate hyaline inclusions. These features suggested a mutation of SOD1 mutation although no other family members were affected. DNA analysis of autopsy tissue indicated an I113T SOD1 mutation.
散发性肌萎缩侧索硬化症(ALS)患者的尸检很少能为遗传病因提供线索。我们研究了一名66岁女性,她在因乳腺癌接受乳房切除和化疗1年后出现进行性肌无力、肌束震颤和上运动神经元体征。她在神经症状出现后14个月死亡。尸检显示有ALS的特征性表现,但也伴有后柱变性和聚集性透明包涵体。这些特征提示存在超氧化物歧化酶1(SOD1)突变,尽管没有其他家庭成员受影响。对尸检组织的DNA分析表明存在SOD1基因I113T突变。