Bonifas J M, Rothman A L, Epstein E H
Department of Dermatology, San Francisco General Hospital, University of California 94110.
Science. 1991 Nov 22;254(5035):1202-5. doi: 10.1126/science.1720261.
Epidermolysis bullosa simplex (EBS) is characterized by skin blistering due to basal keratinocyte fragility. In one family studied, inheritance of EBS is linked to the gene encoding keratin 14, and a thymine to cytosine mutation in exon 6 of keratin 14 has introduced a proline in the middle of an alpha-helical region. In a second family, inheritance of EBS is linked to loci that map near the keratin 5 gene. These data indicate that abnormalities of either of the components of the keratin intermediate filament heterodipolymer can impair the mechanical stability of these epithelial cells.
单纯性大疱性表皮松解症(EBS)的特征是由于基底角质形成细胞脆弱而导致皮肤水疱形成。在一个研究的家族中,EBS的遗传与编码角蛋白14的基因相关,并且角蛋白14外显子6中的胸腺嘧啶到胞嘧啶突变在α螺旋区域中间引入了一个脯氨酸。在另一个家族中,EBS的遗传与定位在角蛋白5基因附近的基因座相关。这些数据表明,角蛋白中间丝异二聚体的任何一个组分异常都可能损害这些上皮细胞的机械稳定性。