Hoffman Ronald, Prchal Josef T, Samuelson Scott, Ciurea Stefan O, Rondelli Damiano
Hematology Oncology Section, Department of Medicine, University of Illinois College of Medicine, Chicago, Illinois 60612, USA.
Biol Blood Marrow Transplant. 2007 Jan;13(1 Suppl 1):64-72. doi: 10.1016/j.bbmt.2006.11.003.
The Philadelphia chromosome (Ph)-negative myeloproliferative disorders (MPDs) include essential thrombocythemia (ET), idiopathic myelofibrosis (IMF), and polycythemia vera (PV). All of these disorders are clonal hematologic malignancies originating at the level of the pluripotent hematopoietic stem cell. Recently, activating mutations of the intracellular cytokine-signaling molecule JAK2 have been identified in > 90% of patients with PV and in 50% of those with IMF and ET. In addition, a mutation of the thrombopoietin receptor, MPLW515L, has been documented in some patients with IMF. Both mutations activate JAK-STAT signaling pathways and likely play a role in disease progression. Both ET and PV are associated with prolonged clinical courses associated with frequent thrombotic and hemorrhagic events, and progression to myelofibrosis and acute leukemia. IMF has a much poorer prognosis and is associated with cytopenias, splenomegaly, extramedullary hematopoiesis, and bone marrow fibrosis. Stratification of risk for the development of complications from Ph-negative MPDs has guided the identification of appropriate therapies for this population. Intermediate/high-risk IMF or myelofibrosis after ET or PV is associated with a sufficiently poor prognosis to justify the use of allogeneic stem cell transplantation, which is capable of curing such patients. Reduced-intensity conditioning in preparation for allogeneic stem cell transplantation has permitted older patients with IMF to undergo transplantation with increasing success.
费城染色体(Ph)阴性骨髓增殖性疾病(MPD)包括原发性血小板增多症(ET)、原发性骨髓纤维化(IMF)和真性红细胞增多症(PV)。所有这些疾病都是起源于多能造血干细胞水平的克隆性血液系统恶性肿瘤。最近,在超过90%的PV患者以及50%的IMF和ET患者中发现了细胞内细胞因子信号分子JAK2的激活突变。此外,在一些IMF患者中记录到血小板生成素受体MPLW515L的突变。这两种突变均激活JAK-STAT信号通路,并可能在疾病进展中起作用。ET和PV都与临床病程延长相关,常伴有血栓形成和出血事件,并进展为骨髓纤维化和急性白血病。IMF的预后要差得多,与血细胞减少、脾肿大、髓外造血和骨髓纤维化有关。对Ph阴性MPD并发症发生风险的分层指导了针对该人群合适治疗方法的确定。ET或PV后出现的中/高危IMF或骨髓纤维化的预后足够差,因此有理由使用异基因干细胞移植,这种方法能够治愈此类患者。为异基因干细胞移植做准备的减低强度预处理使老年IMF患者进行移植的成功率不断提高。