Ortiz-Gómez J R, Souto-Ferro J M
Servicio de Anestesiología y Reanimación, Hospital Garcia Orcoyen, C/ Santa Soria, 22, 31200 Estella, Navarra.
Rev Esp Anestesiol Reanim. 2006 Nov;53(9):575-9.
Mitochondrial myopathies make up a group of rare disorders whose onset is in childhood or adolescence. Muscle and central nervous system involvement is variable. Mitochondrial respiratory chain complex III deficiency (coenzyme Q - cytochrome C reductase) can manifest as exercise intolerance, myopathy, encephalopathy, and myocardial disease. Approximately 38 patients with complex III deficiency have been described since 1966, yet only a single anesthetic experience (epidural analgesia for cesarean delivery) has been reported. We describe the case of an 11-year-old boy with mitochondrial respiratory chain complex III deficiency, severe myopathy, and moderate encephalopathy who underwent surgery to improve right ischiotibial muscle spasticity. Monitoring included electrocardiography, noninvasive blood pressure, oxygen saturation by pulse oximetry, end-tidal carbon dioxide pressure, esophageal temperature, spirometry, and neuromuscular block (Relaxograph Datex). Midazolam, fentanyl, and propofol were used for anesthetic induction; mivacurium was used during intubation. Anesthetic maintenance was with propofol in continuous infusion and fractionated doses of fentanyl and mivacurium on demand in a mixture of oxygen and air. The boy's response to mivacurium was abnormal but he could nevertheless be extubated in the operating room at a train-of-four ratio of 75% and with no need to reverse the neuromuscular blockade. There were no problems during the anesthetic procedure, so it could be a good technique for these patients, despite of considering individually every case and extension of syntomatology, due to the little experience in anesthesia with deficiency of Complex III.
线粒体肌病是一组罕见的疾病,发病于儿童期或青春期。肌肉和中枢神经系统受累情况各不相同。线粒体呼吸链复合物III缺乏症(辅酶Q - 细胞色素C还原酶)可表现为运动不耐受、肌病、脑病和心肌病。自1966年以来,已报道约38例复合物III缺乏症患者,但仅有一例麻醉经验(剖宫产硬膜外镇痛)的报道。我们描述了一名11岁男孩的病例,他患有线粒体呼吸链复合物III缺乏症、严重肌病和中度脑病,接受了手术以改善右侧坐骨胫骨肌痉挛。监测包括心电图、无创血压、脉搏血氧饱和度、呼气末二氧化碳分压、食管温度、肺活量测定和神经肌肉阻滞(Datex Relaxograph)。咪达唑仑、芬太尼和丙泊酚用于麻醉诱导;插管时使用米库氯铵。麻醉维持采用持续输注丙泊酚,并按需分次给予芬太尼和米库氯铵,吸入氧气和空气的混合气体。该男孩对米库氯铵的反应异常,但仍能在手术室以四个成串刺激比值为75%时拔管,且无需逆转神经肌肉阻滞。麻醉过程中未出现问题,因此尽管由于复合物III缺乏症的麻醉经验较少,需要对每个病例和症状的范围进行个别考虑,但这可能是适合这些患者的良好技术。