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Colorectal cancer screening. Clinical practice guidelines in oncology.结直肠癌筛查。肿瘤学临床实践指南。
J Natl Compr Canc Netw. 2003 Jan;1(1):72-93. doi: 10.6004/jnccn.2003.0009.
2
Medulloblastoma, acute myelocytic leukemia and colonic carcinomas in a child with biallelic MSH6 mutations.一名患有双等位基因MSH6突变的儿童患髓母细胞瘤、急性髓细胞白血病和结肠癌。
Nat Clin Pract Oncol. 2007 Feb;4(2):130-4. doi: 10.1038/ncponc0719.
3
A hypermutation phenotype and somatic MSH6 mutations in recurrent human malignant gliomas after alkylator chemotherapy.烷化剂化疗后复发性人类恶性胶质瘤中的高突变表型和体细胞MSH6突变。
Cancer Res. 2006 Apr 15;66(8):3987-91. doi: 10.1158/0008-5472.CAN-06-0127.
4
PMS2 mutations in childhood cancer.儿童癌症中的PMS2突变。
J Natl Cancer Inst. 2006 Mar 1;98(5):358-61. doi: 10.1093/jnci/djj073.
5
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Eur J Hum Genet. 2006 May;14(5):561-6. doi: 10.1038/sj.ejhg.5201568.
6
A novel MSH2 germline mutation in homozygous state in two brothers with colorectal cancers diagnosed at the age of 11 and 12 years.在两名分别于11岁和12岁时被诊断出患有结直肠癌的兄弟中,发现一种纯合状态的新型MSH2种系突变。
Am J Med Genet A. 2006 Feb 1;140(3):195-9. doi: 10.1002/ajmg.a.31070.
7
Mechanisms of therapy-related carcinogenesis.治疗相关致癌作用的机制。
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8
Neurofibromatosis von Recklinghausen type I phenotype and early onset of cancers in siblings compound heterozygous for mutations in MSH6.1型冯雷克林霍增氏神经纤维瘤病表型以及MSH6基因发生突变的复合杂合子同胞中癌症的早发。
Am J Med Genet A. 2005 Dec 1;139A(2):96-105; discussion 96. doi: 10.1002/ajmg.a.30998.
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Early response to induction is predictive of survival in childhood Philadelphia chromosome positive acute lymphoblastic leukaemia: results of the Medical Research Council ALL 97 trial.诱导治疗的早期反应可预测儿童费城染色体阳性急性淋巴细胞白血病的生存率:医学研究委员会ALL 97试验结果
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The impact of the methotrexate administration schedule and dose in the treatment of children and adolescents with B-cell neoplasms: a report of the BFM Group Study NHL-BFM95.甲氨蝶呤给药方案和剂量对儿童及青少年B细胞肿瘤治疗的影响:BFM组NHL-BFM95研究报告
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双等位基因MSH2突变引起的家族性T细胞非霍奇金淋巴瘤。

Familial T-cell non-Hodgkin lymphoma caused by biallelic MSH2 mutations.

作者信息

Scott Richard H, Homfray Tessa, Huxter Nicola L, Mitton Sally G, Nash Ruth, Potter Mike N, Lancaster Donna, Rahman Nazneen

机构信息

Section of Cancer Genetics, Institute of Cancer Research, 15 Cotswold Road, Sutton, Surrey, UK, SM2 5NG.

出版信息

J Med Genet. 2007 Jul;44(7):e83. doi: 10.1136/jmg.2007.048942.

DOI:10.1136/jmg.2007.048942
PMID:17601929
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC2597999/
Abstract

Familial non-Hodgkin lymphoma (NHL) is rare and in most cases, no underlying cause is identifiable. We report homozygous truncating mutations in the mismatch repair gene MSH2 (226C-->T; Q76X) in three siblings who each developed T-cell NHL in early childhood. All three children had hyperpigmented and hypopigmented skin lesions. Constitutional biallelic MSH2 mutations have previously been reported in five individuals, all of whom developed malignancy in childhood. Familial lymphoma has not been reported in this context or in association with biallelic mutations in the other mismatch repair genes MLH1, MSH6 or PMS2. In addition, hypopigmented skin lesions have not previously been reported in biallelic MSH2 carriers. Our findings therefore expand the spectrum of phenotypes associated with biallelic MSH2 mutations and identify a new cause of familial lymphoma. Moreover, the diagnosis has important management implications as it allows the avoidance of chemotherapeutic agents likely to be ineffective and mutagenic in the proband, and the provision of cascade genetic testing and tumour screening for relatives.

摘要

家族性非霍奇金淋巴瘤(NHL)较为罕见,在大多数情况下,无法确定潜在病因。我们报告了三个同胞中错配修复基因MSH2(226C→T;Q76X)的纯合截断突变,这三个同胞均在幼儿期患T细胞NHL。所有三个孩子都有色素沉着过度和色素沉着不足的皮肤病变。此前已报道五例个体存在双等位基因MSH2突变,他们均在儿童期发生恶性肿瘤。在这种情况下,尚未有家族性淋巴瘤的报道,也未发现与其他错配修复基因MLH1、MSH6或PMS2的双等位基因突变有关。此外,此前尚未报道双等位基因MSH2携带者出现色素沉着不足的皮肤病变。因此,我们的研究结果扩展了与双等位基因MSH2突变相关的表型谱,并确定了家族性淋巴瘤的一个新病因。此外,该诊断具有重要的管理意义,因为它可以避免使用可能对先证者无效且具有致突变性的化疗药物,并为亲属提供级联基因检测和肿瘤筛查。