Mason Philip J, Bautista José M, Gilsanz Florinda
Division of Hematology, Department of Internal Medicine, Washington University School of Medicine, Campus Box 8125, 660 South Euclid Avenue, St. Louis, MO 63110, USA.
Blood Rev. 2007 Sep;21(5):267-83. doi: 10.1016/j.blre.2007.05.002. Epub 2007 Jul 3.
Deficiency of glucose-6-phosphate dehydrogenase is a very common X-linked genetic disorder though most deficient people are asymptomatic. A number of different G6PD variants have reached polymorphic frequencies in different parts of the world due to the relative protection they confer against malaria infection. People, usually males, with deficient alleles are susceptible to neonatal jaundice, and acute hemolytic anemia, usually during infection, after treatment with certain drugs or after eating fava beans. Very rarely de novo mutations can arise causing the more severe condition of chronic nonspherocytic hemolytic anemia. Altogether 160 different mutations have been described. The majority of mutations cause red cell enzyme deficiency by decreasing enzyme stability. The polymorphic mutations affect amino acid residues throughout the enzyme and decrease the stability of the enzyme in the red cell, possibly by disturbing protein folding. The severe mutations mostly affect residues at the dimer interface or those that interact with a structural NADP molecule that stabilizes the enzyme.
葡萄糖-6-磷酸脱氢酶缺乏症是一种非常常见的X连锁遗传病,不过大多数缺乏该酶的人没有症状。由于一些不同的G6PD变体对疟疾感染具有相对保护作用,它们在世界不同地区已达到多态频率。携带缺陷等位基因的人,通常为男性,易患新生儿黄疸和急性溶血性贫血,通常在感染期间、使用某些药物治疗后或食用蚕豆后发病。非常罕见的情况下会出现新发突变,导致更严重的慢性非球形细胞溶血性贫血。总共已描述了160种不同的突变。大多数突变通过降低酶的稳定性导致红细胞酶缺乏。多态性突变影响整个酶的氨基酸残基,并可能通过干扰蛋白质折叠降低红细胞中酶的稳定性。严重突变大多影响二聚体界面处的残基或与稳定酶的结构NADP分子相互作用的残基。