Kersnik Levart Tanja
Department of Pediatric Nephrology, University Medical Center, Stare pravde 4, 1000 Ljubljana, Slovenia.
Pediatr Nephrol. 2007 Nov;22(11):1975-8. doi: 10.1007/s00467-007-0566-3. Epub 2007 Aug 7.
Lesch-Nyhan syndrome is a very rare X-linked recessive disorder characterized by mental retardation, spasticity resembling cerebral palsy, choreo-athetosis, self-mutilation and hyperuricemia. Self-mutilative behavior is a hallmark of the disease. Hyperuricemia leads to hyperuricuria and uric acid nephrolithiasis. The underlying defect is a deficiency of hypoxanthine-guanine-phosphoribosyl transferase. We report on a 7-year-old boy with Lesch-Nyhan syndrome, lacking self-mutilative behavior, who was erroneously diagnosed as having athetotic cerebral palsy. He also had no renal stones; hyperechoic renal medullary pyramids were the only renal abnormality detected and were sonographically indistinguishable from medullary nephrocalcinosis.
莱施-奈恩综合征是一种非常罕见的X连锁隐性疾病,其特征为智力发育迟缓、类似脑瘫的痉挛状态、舞蹈手足徐动症、自残行为和高尿酸血症。自残行为是该疾病的一个标志。高尿酸血症会导致高尿酸尿症和尿酸肾结石。潜在缺陷是次黄嘌呤-鸟嘌呤-磷酸核糖转移酶缺乏。我们报告了一名7岁患有莱施-奈恩综合征的男孩,他没有自残行为,曾被误诊为手足徐动型脑瘫。他也没有肾结石;肾髓质锥体高回声是唯一检测到的肾脏异常,在超声检查中与髓质肾钙质沉着症无法区分。