Sotlar Karl
Institut für Pathologie, Universität Tübingen.
Verh Dtsch Ges Pathol. 2006;90:227-35.
Detection of activating c-kit mutation D816 V is one of five criteria for the diagnosis of systemic mastocytosis (SM). The aims of this study were to (I) establish molecular methods for the detection of these mutations in paraffin-embedded biopsies, (II) determine the frequency of these mutations in mastocytoses and control tissues, (III) determine the frequency of these mutations in laser-microdissected lesional and nonlesional mast cells (MC), and (IV) investigate these matutions as a marker for clonality in cases with SM and associated clonal hematologic non-mast cell lineage diseases (SM-AHNMD). Formalin-fixed and paraffin-embedded biopsies of 48 patients with cutaneous mastocytosis (CM), 55 cases with various forms of SM, and 239 controls were investigated by PNA-mediated PCR-clamping. In addition, nested PCR amplified DNA of pooled microdissected single mast cells (MC) was investigated by melting point analysis. Activating c-kit mutation codon 816 mutations were detected in 38 % (18/48) of CM, in 91% (50/55) of SM, in 5 % (2/39) of MC hyperplasia and in none of 200 hematologic non-MC neoplasias. c-kit mutations were detected significantly more frequent in lesional MC as compared to non-lesional MC (p = 0,003). In 6/15 (40 %) cases with SM-AHNMD the same c-kit mutations were detected in microdissected MC and AHNMD cells. This study underlines the concept of the actual WHO classification of mastocytoses. By establishing methods for the detection of c-kit codon 816 mutations in paraffin-embedded tissues, the pathologist holds a central position in the diagnosis of systemic mastocytoses.
检测激活型c-kit突变D816V是系统性肥大细胞增多症(SM)诊断的五项标准之一。本研究的目的是:(I)建立在石蜡包埋活检组织中检测这些突变的分子方法;(II)确定这些突变在肥大细胞增多症和对照组织中的频率;(III)确定这些突变在激光显微切割的病变和非病变肥大细胞(MC)中的频率;(IV)研究这些突变作为SM及相关克隆性血液非肥大细胞谱系疾病(SM-AHNMD)病例中克隆性的标志物。采用肽核酸(PNA)介导的PCR钳夹技术对48例皮肤肥大细胞增多症(CM)患者、55例各种形式的SM患者和239例对照的福尔马林固定石蜡包埋活检组织进行研究。此外,通过熔点分析对巢式PCR扩增的汇集显微切割单个肥大细胞(MC)的DNA进行研究。在CM患者中,38%(18/48)检测到激活型c-kit突变密码子816突变;在SM患者中,91%(50/55)检测到该突变;在MC增生患者中,5%(2/39)检测到该突变;在200例血液非MC肿瘤中均未检测到该突变。与非病变MC相比,病变MC中c-kit突变的检测频率显著更高(p = 0.003)。在6/15(40%)例SM-AHNMD病例中,在显微切割的MC和AHNMD细胞中检测到相同的c-kit突变。本研究强调了世界卫生组织(WHO)现行肥大细胞增多症分类的概念。通过建立在石蜡包埋组织中检测c-kit密码子816突变的方法,病理学家在系统性肥大细胞增多症的诊断中占据核心地位。